Verma Arpana, Rajbhar Sarita, Thakur Pushpawati, Agrawal Sarita, Pradhan Sangeeta
Department of Obstetrics and Gynecology, All India Institute of Medical Sciences, Raipur, Chhattisgarh 492099, India.
J Med Cases. 2021 Jan;12(1):27-31. doi: 10.14740/jmc3610. Epub 2020 Nov 18.
To present a case of successful pregnancy outcome in a granulomatosis with polyangiitis (GPA) patient with renal insufficiency. GPA, formerly known as Wegener's granulomatosis, is a rare necrotizing systemic vasculitis, presenting with classical clinical triad of manifestations involving upper and lower airway and glomerulonephritis. An association of Antineutrophil cytoplasmic antibodies with GPA has been established and the antibodies are present in most patients with active disease. Pregnancy with GPA is burdened with the risk of possible maternal and fetal complications, further leading to higher morbidity and mortality rate. Due to sparsity of studies of GPA in pregnancy, management needs to be individualised. Diagnostic workup should include serological markers, radiological and histopathological examination. Cyclophosphamide combined with prednisolone is the standard induction regimen. A 22-year-old woman, multigravida at 35 weeks of gestation was referred to our department owing to 1-year diagnosis of GPA. During active phase, the disease manifested as pneumonia and acute kidney injury and perinuclear anti-neutrophil cytoplasmic antibodies (P-ANCAs) were positive. She received pulse therapy of injection cyclophosphamide and methylprednisolone as induction regimen, followed by tapering doses of oral prednisolone and azathioprine for maintenance therapy. The disease was in remission at the onset of pregnancy but had flare up at 34 - 35 weeks of gestation and she presented with renal dysfunction. Neither the disease nor the treatment adversely affected the pregnancy and she delivered a healthy baby at 37 weeks. The unpredictable disease course and complications at unexpected gestation appears to be a major variable to take into account when assessing the risk of pregnancy with GPA. Early diagnosis, monitoring and timely intervention resulted in favourable pregnancy outcome in our patient.
报告一例肉芽肿性多血管炎(GPA)合并肾功能不全患者成功妊娠的病例。GPA既往称为韦格纳肉芽肿,是一种罕见的坏死性系统性血管炎,具有涉及上、下呼吸道及肾小球肾炎的典型临床三联征表现。抗中性粒细胞胞浆抗体与GPA的关联已被确立,且大多数活动期患者体内存在该抗体。GPA患者妊娠存在母婴并发症的风险,进而导致更高的发病率和死亡率。由于关于GPA妊娠的研究较少,管理需个体化。诊断检查应包括血清学标志物、影像学及组织病理学检查。环磷酰胺联合泼尼松龙是标准的诱导方案。一名22岁的经产妇,妊娠35周,因确诊GPA 1年转诊至我科。活动期时,疾病表现为肺炎和急性肾损伤,核周型抗中性粒细胞胞浆抗体(P-ANCA)呈阳性。她接受了注射用环磷酰胺和甲泼尼龙的脉冲治疗作为诱导方案,随后逐渐减量口服泼尼松龙和硫唑嘌呤进行维持治疗。妊娠开始时疾病处于缓解期,但在妊娠34 - 35周时病情复发,出现肾功能不全。疾病及治疗均未对妊娠产生不利影响,她在37周时分娩了一个健康的婴儿。在评估GPA患者妊娠风险时,不可预测的病程及意外妊娠时的并发症似乎是一个需要考虑的主要变量。早期诊断、监测及及时干预使我们的患者获得了良好的妊娠结局。