Pantoja Letícia L Quirino, Lustosa Mariana, Yamaguti Paulo Márcio, Rosa Lídia S, Leite André Ferreira, Figueiredo Paulo Tadeu S, Castro Luiz Claudio, Acevedo Ana Carolina
Oral Care Center for Inherited Diseases, University of Brasília, Brasília, DF, Brazil.
Laboratory of Oral Histopathology, Faculty of Healthy Science, University of Brasília, Brasília, DF, Brazil.
Calcif Tissue Int. 2022 Mar;110(3):303-312. doi: 10.1007/s00223-021-00915-3. Epub 2021 Oct 22.
Patients with Osteogenesis Imperfecta (OI) present extra-skeletal manifestations, including important orodental and craniofacial features as dentinogenesis imperfecta, dental agenesis, failure of maxilla growth and hypotonia of masticatory muscles. These features may compromise vital functions speech and mastication. Studies have demonstrated that cyclic pamidronate infusion, the standard therapy for patients with moderate to severe OI, influences the histomorphometric pattern of different body bones. The present study aimed to investigate the condyle trabecular bone pattern in OI patients. We used fractal dimension (FD) analysis on dental panoramic radiographic images to characterize the mandibular condyle trabecular bone in adolescents diagnosed with OI and treated with pamidronate. Imaging exam of 33 adolescents of both sexes, aged between 12 and 17 years, were analyzed and compared with 99 age- and sex-matched healthy adolescents. FD in patients was significantly lower (1.23 ± 0.15) than in healthy controls (1.29 ± 0.11; p < 0.01). Type of OI, age at treatment onset, and the duration of therapy were variables that showed a statistically significant effect on the FD results. This study demonstrated that the bone architecture of mandibular condyles may be altered in pediatric patients with moderate and severe forms of OI. Also, pamidronate treatment seems to have a positive effect on condyle trabecular bone in these patients. This is supported by our finding that FD values were positively influenced by the length of cyclic pamidronate treatment at the time of imaging, as well as by the age of the individual at treatment onset.
成骨不全症(OI)患者存在骨骼外表现,包括重要的口腔和颅面特征,如牙本质发育不全、牙齿缺失、上颌骨生长障碍和咀嚼肌低张力。这些特征可能会损害言语和咀嚼等重要功能。研究表明,环磷酰胺输注作为中重度OI患者的标准治疗方法,会影响不同身体骨骼的组织形态计量模式。本研究旨在调查OI患者的髁突小梁骨模式。我们对牙科全景X线图像进行分形维数(FD)分析,以表征诊断为OI并接受帕米膦酸盐治疗的青少年的下颌髁突小梁骨。对33名年龄在12至17岁之间的青少年进行成像检查,并与99名年龄和性别匹配的健康青少年进行分析和比较。患者的FD值(1.23±0.15)显著低于健康对照组(1.29±0.11;p<0.01)。OI类型、治疗开始年龄和治疗持续时间是对FD结果有统计学显著影响的变量。本研究表明,中度和重度OI患儿的下颌髁突骨结构可能会发生改变。此外,帕米膦酸盐治疗似乎对这些患者的髁突小梁骨有积极作用。我们的研究结果支持了这一点,即成像时环磷酰胺治疗的时长以及治疗开始时个体的年龄对FD值有积极影响。