Wu Jinchun, Hu Yongbin, Abdihamid Omar, Huang Gengwen, Xiao Sheng, Li Bin
Department of Oncology, Xiangya Hospital, Central South University, Changsha, China.
Department of Pathology, Xiangya Hospital, Central South University, Changsha, China.
Front Oncol. 2021 Oct 14;11:684865. doi: 10.3389/fonc.2021.684865. eCollection 2021.
Sarcoma or sarcomatoid malignancies are a set of mesenchymal-origin malignancies with vast heterogeneity in clinical and molecular characteristics. Anaplastic lymphoma kinase (ALK) is a tyrosine kinase oncoprotein expressed by several tumors, including sarcomas. Crizotinib is an effective ALK inhibitor. In this review paper, we summarized findings from the literature regarding the use of crizotinib for the treatment of sarcoma and sarcomatoid malignancies harboring ALK fusions with definitive partners (with the given gene(s) name) from the years 2010 to 2021.One hundred and four articles were retrieved and after exclusion, 28 studies containing 33 patients were finally selected. All 33 patients were treated with crizotinib. Among the 33 cases, 19 were adult patients, 11 were pediatric patients, and 3 cases did not have data on age and/or gender. Most cases had a primary abdominal lesion (16/30), followed by thoracic (10/30), trunk (3/30), retroperitoneal (1/30), and one case of right medial thigh (case 7). Stage IV disease was reported in 76.7% (23/30) of patients. The objective response rate and disease control rate was 86.7% (26/30) and 96.7% (29/30), respectively, which were assessed on average of 8 weeks after crizotinib initiation. Rapid improvement of symptoms was observed within one to two weeks in some cases including patients with extensive diseases or poor performance. There was no difference in crizotinib response between pediatrics and adult cases. Crizotinib is effective; however, surgery remains the mainstay of therapy, with newer evidence showing concurrent crizotinib with surgery conferring long-term overall survival. However, we should still be cognizant of the heterogeneous landscape of crizotinib efficacy and its associated fatal adverse events.
肉瘤或肉瘤样恶性肿瘤是一组起源于间充质的恶性肿瘤,在临床和分子特征上具有很大的异质性。间变性淋巴瘤激酶(ALK)是一种由多种肿瘤(包括肉瘤)表达的酪氨酸激酶癌蛋白。克唑替尼是一种有效的ALK抑制剂。在这篇综述论文中,我们总结了2010年至2021年期间关于使用克唑替尼治疗携带与明确伙伴(给出基因名称)发生ALK融合的肉瘤和肉瘤样恶性肿瘤的文献研究结果。检索到104篇文章,排除后最终选择了28项研究,共33例患者。所有33例患者均接受了克唑替尼治疗。在这33例病例中,19例为成年患者,11例为儿科患者,3例没有年龄和/或性别的数据。大多数病例有原发性腹部病变(16/30),其次是胸部(10/30)、躯干(3/30)、腹膜后(1/30),还有1例右大腿内侧病例(病例7)。76.7%(23/30)的患者报告为IV期疾病。客观缓解率和疾病控制率分别为86.7%(26/30)和96.7%(29/30),在开始使用克唑替尼后平均8周进行评估。在一些病例中,包括患有广泛疾病或身体状况较差的患者,在1至2周内观察到症状迅速改善。儿科病例和成年病例在克唑替尼反应方面没有差异。克唑替尼是有效的;然而,手术仍然是主要的治疗方法,新的证据表明克唑替尼与手术同时使用可带来长期总生存。然而,我们仍应认识到克唑替尼疗效的异质性及其相关的致命不良事件。