Department of Degenerative Neurological Diseases, National Institute of Neuroscience, National Center of Neurology and Psychiatry, 4-1-1 Ogawa-Higashi, Kodaira, Tokyo, 187-8502, Japan.
Department of Pathology and Laboratory Medicine, National Center Hospital, National Center of Neurology and Psychiatry, Tokyo, Japan.
Neurochem Int. 2022 Jan;152:105243. doi: 10.1016/j.neuint.2021.105243. Epub 2021 Nov 18.
Parkinson's disease (PD) and dementia with Lewy bodies (DLB) are major neurodegenerative disorders that share commonalities in their pathology involving the formation of Lewy bodies, the main component of which is α-synuclein protein. Aberrancy and dysfunction in lysosomes have been suggested to play critical roles in the pathogenesis of Lewy body diseases. We recently identified a novel lysosomal degradation pathway in which various macromolecules, including α-synuclein protein, are directly imported into lysosomes and degraded. In this study, we analyzed the levels and localization of the lysosomal membrane protein SIDT2, a key factor in this pathway, in the postmortem brains of patients with PD and DLB. The levels of SIDT2 protein were significantly higher in the anterior cingulate cortex (ACC) of both PD and DLB cases than in age-matched control subjects, but this difference was not observed in the inferior frontal gyrus. The levels of SIDT2 also showed a strong correlation with α-synuclein levels in the ACC of all subjects, including controls. SIDT2 was colocalized with aggregates positive for phosphorylated α-synuclein protein, which is a hallmark of Lewy bodies, in all examined cases of both PD and DLB. These observations suggest that changes in the levels and localization of SIDT2 occur at the lesion site of Lewy body diseases in accordance with the progression of Lewy body pathology. Our findings provide mechanistic insights into the pathogenesis of Lewy body diseases, as well as other neurodegenerative disorders, and may provide clues for improved diagnosis, prevention, and therapeutic intervention for such diseases.
帕金森病(PD)和路易体痴呆(DLB)是两种主要的神经退行性疾病,它们在病理学上有共同之处,涉及路易体的形成,而路易体的主要成分是α-突触核蛋白。溶酶体的异常和功能障碍被认为在路易体疾病的发病机制中起着关键作用。我们最近发现了一种新的溶酶体降解途径,其中包括α-突触核蛋白在内的各种大分子可以直接被导入溶酶体并降解。在这项研究中,我们分析了 PD 和 DLB 患者死后大脑中溶酶体膜蛋白 SIDT2 的水平和定位,SIDT2 是该途径的关键因素。PD 和 DLB 病例的前扣带回皮层(ACC)中 SIDT2 蛋白水平明显高于年龄匹配的对照组,但在下额回中未观察到这种差异。SIDT2 水平与所有受试者(包括对照组)ACC 中的α-突触核蛋白水平也呈强烈相关。在所有 PD 和 DLB 检查病例中,SIDT2 与磷酸化α-突触核蛋白阳性的聚集体共定位,磷酸化α-突触核蛋白是路易体的标志。这些观察结果表明,SIDT2 的水平和定位的变化与路易体病理学的进展相一致,发生在路易体疾病的病变部位。我们的发现为路易体疾病以及其他神经退行性疾病的发病机制提供了机制上的见解,并可能为这些疾病的改进诊断、预防和治疗干预提供线索。