Department of Biochemistry, Institute of Hematology and Blood Transfusion, U Nemocnice 1, 12800 Prague, Czech Republic.
Int J Mol Sci. 2021 Dec 23;23(1):132. doi: 10.3390/ijms23010132.
Fibrinogen, an abundant plasma glycoprotein, is involved in the final stage of blood coagulation. Decreased fibrinogen levels, which may be caused by mutations, are manifested mainly in bleeding and thrombotic disorders. Clinically relevant mutations of fibrinogen are listed in the Human Fibrinogen Database. For the αC-connector (amino acids Aα240-410, nascent chain numbering), we have extended this database, with detailed descriptions of the clinical manifestations among members of reported families. This includes the specification of bleeding and thrombotic events and results of coagulation assays. Where available, the impact of a mutation on clotting and fibrinolysis is reported. The collected data show that the Human Fibrinogen Database reports considerably fewer missense and synonymous mutations than the general COSMIC and dbSNP databases. Homozygous nonsense or frameshift mutations in the αC-connector are responsible for most clinically relevant symptoms, while heterozygous mutations are often asymptomatic. Symptomatic subjects suffer from bleeding and, less frequently, from thrombotic events. Miscarriages within the first trimester and prolonged wound healing were reported in a few subjects. All mutations inducing thrombotic phenotypes are located at the identical positions within the consensus sequence of the tandem repeats.
纤维蛋白原是一种丰富的血浆糖蛋白,参与血液凝固的最后阶段。纤维蛋白原水平降低可能由突变引起,主要表现为出血和血栓形成障碍。纤维蛋白原的临床相关突变已被列入人类纤维蛋白原数据库。对于 αC-连接子(氨基酸 Aα240-410,新生链编号),我们已经扩展了这个数据库,详细描述了报告家族成员的临床表现。这包括出血和血栓形成事件的说明以及凝血测定的结果。在可用的情况下,报告了突变对凝血和纤维蛋白溶解的影响。收集的数据表明,人类纤维蛋白原数据库报告的错义和同义突变明显少于一般的 COSMIC 和 dbSNP 数据库。αC-连接子中的纯合无义或移码突变导致大多数临床相关症状,而杂合突变通常无症状。有症状的患者会出现出血,较少出现血栓形成事件。少数患者报告有早期流产和伤口愈合延长。所有诱导血栓形成表型的突变都位于串联重复的共识序列中的相同位置。