Division of Nephrology, Department of Medicine, Center for Immunity, Inflammation and Regenerative Medicine (CIIR), University of Virginia, Charlottesville, Virginia, United States.
Department of Biochemistry, Center for Structural Biology, Wake Forest University School of Medicine, Winston-Salem, North Carolina, United States.
Eur J Immunol. 2022 May;52(5):825-834. doi: 10.1002/eji.202149324. Epub 2022 Feb 15.
The Three Prime Repair EXonuclease I (TREX1) is critical for degrading post-apoptosis DNA. Mice expressing catalytically inactive TREX1 (TREX1 D18N) develop lupus-like autoimmunity due to chronic sensing of undegraded TREX1 DNA substrates, production of the inflammatory cytokines, and the inappropriate activation of innate and adaptive immunity. This study aimed to investigate Thelper (Th) dysregulation in the TREX1 D18N model system as a potential mechanism for lupus-like autoimmunity. Comparison of immune cells in secondary lymphoid organs, spleen and peripheral lymph nodes (LNs) between TREX1 D18N mice and the TREX1 null mice revealed that the TREX1 D18N mice exhibit a Th1 bias. Additionally, the T-follicular helper cells (Tfh) and the germinal celter (GC) B cells were also elevated in the TREX1 D18N mice. Targeting Bcl6, a lineage-defining transcription factor for Tfh and GC B cells, with a commercially available Bcl6 inhibitor, FX1, attenuated Tfh, GC, and Th1 responses, and rescued TREX1 D18N mice from autoimmunity. The study presents Tfh and GC B-cell responses as potential targets in autoimmunity and that Bcl6 inhibitors may offer therapeutic approach in TREX1-associated or other lupus-like diseases.
三引物修复外切核酸酶 I(TREX1)对于降解凋亡后 DNA 至关重要。表达无催化活性 TREX1(TREX1 D18N)的小鼠由于未降解的 TREX1 DNA 底物的慢性感知、炎性细胞因子的产生以及先天和适应性免疫的不适当激活,会发展出狼疮样自身免疫。本研究旨在探讨 TREX1 D18N 模型系统中辅助性 T 细胞(Th)失调作为狼疮样自身免疫的潜在机制。比较 TREX1 D18N 小鼠和 TREX1 缺失小鼠次级淋巴器官、脾脏和外周淋巴结(LNs)中的免疫细胞,结果显示 TREX1 D18N 小鼠表现出 Th1 偏向。此外,T 滤泡辅助细胞(Tfh)和生发中心 B 细胞(GC B 细胞)在 TREX1 D18N 小鼠中也升高。用商业上可用的 Bcl6 抑制剂 FX1 靶向 Bcl6,一种 Tfh 和 GC B 细胞的谱系定义转录因子,可减弱 Tfh、GC 和 Th1 反应,并使 TREX1 D18N 小鼠免于自身免疫。该研究提出 Tfh 和 GC B 细胞反应是自身免疫的潜在靶点,并且 Bcl6 抑制剂可能为 TREX1 相关或其他狼疮样疾病提供治疗方法。