Department of Neurology, Calcutta National Medical College & Hospital, Kolkata, West Bengal, India.
Department of Neurology, University Hospital "12 de Octubre", Madrid, Spain; Centro de Investigación Biomédica en Red sobre Enfermedades Neurodegenerativas (CIBERNED), Madrid, Spain; Department of Medicine, Complutense University, Madrid, Spain.
J Neuroimmunol. 2022 May 15;366:577844. doi: 10.1016/j.jneuroim.2022.577844. Epub 2022 Mar 9.
Primary angiitis of the central nervous system is a rare disease characterized by vasculitis of the central nervous system without any systemic involvement. This review aims to provide an insight into the existing stagnancies in the diagnostic approach and management of this disease. The clinical presentation is typically nonspecific, ranging from headaches, altered sensorium, and seizures to recurrent ischemic strokes. The definitive diagnosis can only be ascertained by histopathological studies of tissue obtained from a brain biopsy. While angiography can provide clues to diagnosis, it has often been normal, even in biopsy-proven cases. Primary angiitis of the central nervous system continues to be a diagnostic challenge as little progress has been made over the years in the diagnosis and management strategies. Considering the vast list of mimickers of primary angiitis of the central nervous system and the existence of a significant proportion of imaging-negative and biopsy-negative cases, it becomes imperative to devise universally accepted diagnostic criteria for this disease. Steroids in combination with cyclophosphamide are the agents used to achieve remission. Rituximab can be an alternative. The treatment-related toxicity of cyclophosphamide warrants larger trials for alternative drugs to be studied.
原发性中枢神经系统血管炎是一种罕见的疾病,其特征为中枢神经系统血管炎而无任何系统性受累。本综述旨在深入了解该疾病诊断方法和治疗方面存在的固有难题。其临床表现通常是非特异性的,从头痛、意识改变和癫痫发作到反复发作的缺血性中风不等。只有通过从脑活检获得的组织的组织病理学研究才能确定明确的诊断。虽然血管造影可以提供诊断线索,但即使在活检证实的病例中,血管造影也常常正常。由于在过去几年中,原发性中枢神经系统血管炎的诊断和治疗策略几乎没有取得任何进展,因此原发性中枢神经系统血管炎仍然是一个诊断难题。考虑到原发性中枢神经系统血管炎的大量类似物,以及存在相当比例的影像学阴性和活检阴性病例,制定该疾病的普遍接受的诊断标准变得至关重要。类固醇联合环磷酰胺是用于缓解疾病的药物。利妥昔单抗可以作为替代药物。环磷酰胺的治疗相关毒性需要进行更大规模的试验,以研究替代药物。