Department of Respiratory Medicine, National Hospital Organization Yonago Medical Center, Japan.
Center for Clinical Residency Program, National Hospital Organization Yonago Medical Center, Japan.
Intern Med. 2022 Nov 1;61(21):3287-3291. doi: 10.2169/internalmedicine.9092-21. Epub 2022 Mar 26.
Primary Sjögren's syndrome (pSS) has multi-dimensional manifestations, including neutropenia and polyneuropathy. We herein report a 76-year-old woman with pSS initially presenting as severe granulocyte-colony-stimulating factor (G-CSF)-refractory neutropenia and axonal sensorimotor polyneuropathies (SMP). Systemic glucocorticoid administration had reduced neutrophil-associated immunoglobulin G (NAIgG) on the neutrophil surface as detected using flow cytometry, resulting in the development of neutropenia. A patient with pSS concomitant with axonal SMP might show severe neutropenia as aggressive autoimmune disease. Neutropenia can be treated with systemic glucocorticoids based on the assessment of NAIgG on the neutrophil surface.
原发性干燥综合征(pSS)具有多维度的表现,包括中性粒细胞减少和多发性神经病。本文报告了一例 76 岁女性,最初表现为严重的粒细胞集落刺激因子(G-CSF)难治性中性粒细胞减少症和轴索性感觉运动多发性神经病(SMP)。使用流式细胞术检测到系统性糖皮质激素治疗降低了中性粒细胞表面相关免疫球蛋白 G(NAIgG),导致中性粒细胞减少症的发生。pSS 伴轴索性 SMP 的患者可能表现为严重的中性粒细胞减少症,这是一种侵袭性自身免疫性疾病。根据中性粒细胞表面 NAIgG 的评估,可以用全身性糖皮质激素治疗中性粒细胞减少症。