Royal North Shore Hospital, St Leonards, New South Wales, Australia.
Diagnostic Genomics, PathWest Laboratory Medicine Western Australia, Nedlands, Western Australia, Australia.
BMJ Case Rep. 2022 Mar 30;15(3):e248297. doi: 10.1136/bcr-2021-248297.
An elderly man in his early 80s presented with a 6-month history of worsening lower limb weakness on a background of a longer-standing waddling gait. Examination revealed bilateral scapular winging, and weakness in his proximal and distal lower limbs. Electromyography showed widespread chronic partial denervation changes, while sensory and motor nerve conduction parameters were preserved. After little progression over the course of 18 months, motor neuron disease was deemed less likely. Genetic testing revealed BICD2-related spinal muscular atrophy with lower extremity dominance (SMALED2), a disease that is usually of earlier onset. He is the oldest patient in the literature to be diagnosed with SMALED2 while maintaining ambulation, suggesting the milder spectrum of BICD2-related disease.
一位 80 岁出头的老年男性,在长期蹒跚步态的基础上出现下肢无力进行性加重 6 个月。检查发现双侧肩胛骨翼状,近端和远端下肢无力。肌电图显示广泛的慢性部分去神经改变,而感觉和运动神经传导参数正常。18 个月的病程中几乎没有进展,运动神经元病的可能性较小。基因检测显示 BICD2 相关的以下肢为主的脊髓性肌萎缩症(SMALED2),该病通常发病较早。他是文献中诊断为 SMALED2 而仍能行走的最年长患者,提示 BICD2 相关疾病的较轻谱。