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伴有剑击状硬皮病的帕里-龙贝格病：托珠单抗对牙周骨炎症的影响。

Parry Romberg disease with En Coup de Sabre Scleroderma: Effect of tocilizumab on periodontal bone inflammation.

作者信息

Meneghetti Thaís Cugler, da Silva Juliana Yassue Barbosa, Kluppel Lúcio Eduardo, de Carvalho Vânia Oliveira

机构信息

Unit of Pediatric Rheumatology, Waldemar Monastier Children's Hospital and Clinics Hospital, Federal University of Paraná, Curitiba, Brazil.

Positivo University, Curitiba, Brazil.

出版信息

J Scleroderma Relat Disord. 2021 Jun;6(2):206-210. doi: 10.1177/2397198320975872. Epub 2020 Nov 25.

DOI:10.1177/2397198320975872
PMID:35386743
原文链接:https://pmc.ncbi.nlm.nih.gov/articles/PMC8892937/
Abstract

Parry Romberg disease and En Coupe de Sabre Scleroderma are frequently associated disorders that affect the face and can cause severe aesthetic and functional impairment. Systemic immunosuppression is the gold standard of first-line treatment in the pediatric rheumatology standpoint although it is often delayed in the pediatric dermatology clinics and more often used in cases of refractory neurological impairment. We report on a case with dental root resorption and severe periodontal bone inflammation detected on magnetic resonance imaging, which was successfully treated with the anti-IL-6 agent tocilizumab.

摘要

帕里-龙贝格病和剑状硬皮病是常伴发的疾病，会累及面部，可导致严重的美观和功能损害。从儿科风湿病学角度来看，全身免疫抑制是一线治疗的金标准，尽管在儿科皮肤科诊所这种治疗常常延迟，且更多用于难治性神经功能损害的病例。我们报告了一例磁共振成像检测到牙根吸收和严重牙周骨炎症的病例，该病例用抗白细胞介素-6药物托珠单抗成功治疗。

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