Department of Pediatrics, St. Luke's International Hospital, Tokyo, Japan.
Department of Pediatrics, Shiga University of Medical Science, Seta Tsukinowa-Cho, Otsu, Japan.
Int J Hematol. 2022 Sep;116(3):434-441. doi: 10.1007/s12185-022-03357-1. Epub 2022 May 6.
Although clinical trials have reported an improvement in the prognosis of hemophagocytic lymphohistiocytosis (HLH), current treatment outcomes are unsatisfactory, especially in severe cases. Most clinical trial patients with severe disease discontinue participation due to complications associated with HLH or treatment-related toxicity. A retrospective survey of patients who discontinued participation in the JPLSG HLH-2004 clinical trial was conducted to review the detailed course of these cases to optimize HLH treatment and supportive care. Findings in these patients were compared with those of 45 patients who completed the protocol treatment. The 3 year overall survival rate of patients who completed treatment was 86.7%, versus 50.7% for those who did not complete treatment. Incidence of serious adverse events, such as infections, coagulopathy, and posterior reversible encephalopathy syndrome, during the initial 8 weeks of treatment was much higher in patients who did not complete treatment than in patients who completed treatment. To improve overall outcomes of patients with HLH, it is important to not only optimize HLH-directed therapy but also provide appropriate supportive care.
尽管临床试验报告称噬血细胞性淋巴组织细胞增生症(HLH)的预后有所改善,但目前的治疗效果仍不尽如人意,尤其是在重症病例中。大多数患有严重疾病的临床试验患者因与 HLH 相关的并发症或治疗相关的毒性而停止参与。对退出 JPLSG HLH-2004 临床试验的患者进行了回顾性调查,以回顾这些病例的详细过程,从而优化 HLH 的治疗和支持性护理。将这些患者的发现与完成方案治疗的 45 名患者进行了比较。完成治疗的患者 3 年总生存率为 86.7%,而未完成治疗的患者为 50.7%。在治疗的最初 8 周内,未完成治疗的患者发生严重不良事件(如感染、凝血障碍和后部可逆性脑病综合征)的发生率明显高于完成治疗的患者。为了提高 HLH 患者的总体预后,不仅要优化 HLH 靶向治疗,还要提供适当的支持性护理。