Department of Pediatrics, University College of Medical Sciences and Guru Teg Bahadur Hospital, Dilshad Garden, New Delhi, 110095, India.
Department of Radiodiagnosis, University College of Medical Sciences and Guru Teg Bahadur Hospital, Dilshad Garden, New Delhi 110095, India.
J Trop Pediatr. 2022 Apr 5;68(3). doi: 10.1093/tropej/fmac039.
Low dose factor VIII prophylactic therapy in hemophilia has not been well established till date. This randomized controlled trial compared the efficacy of twice vs. thrice weekly schedule of low dose prophylactic factor VIII in children with hemophilia A as evaluated by the bleeding rate and clinico-radiological evaluation.
Thirty-three children with severe hemophilia A (≤18 years) were randomized into two groups. Baseline evaluation included detailed history, clinical (HJHS 2.1 score and FISH score) and radiological examination (Pettersson score and ultrasound score). Group 1 received twice weekly factor VIII prophylaxis while group 2 received thrice weekly factor VIII prophylaxis, the dose being 10 U/kg in both groups. All participants were followed up over next 6 months to one year. Data regarding acute bleeding episodes and repeat clinico-radiological assessment at the end of follow up were recorded.
We analyzed 14 children in twice weekly prophylaxis group and 16 children in thrice weekly prophylaxis group. Statistically insignificant difference was found between the bleeding rates in both the groups after prophylaxis with the median values of monthly bleeding rate being 0.17 and p-value of 0.79. The differences between the initial and final clinical and radiological scores within each group were found to be statistically significant. There was no significant difference in the clinical and radiological scores in between the groups.
Twice weekly FVIII therapy is effective, easily administered prophylactic schedule to prevent long-term complications of hemophilia A. Lay summaryHemophilia A is one of the most common congenital coagulation factor deficiencies. Low dose factor VIII prophylaxis is recommended for hemophilia in resource-poor settings to reduce the bleeding episodes and improve the quality of life, although the optimal schedule for the same has not been well established. A randomized controlled trial on 33 children with hemophilia A (≤18 years) was done to compare the efficacy of twice versus thrice weekly schedule of prophylactic factor VIII. Group 1 received twice weekly factor VIII prophylaxis while group 2 received thrice weekly factor VIII prophylaxis, the dose in both groups being 10 U/kg. They were evaluated by the bleeding rate and clinical (HJHS 2.1 score and FISH score) and radiological scores (Pettersson score and ultrasound score). All participants were followed up over next 6 months to one year. Data regarding acute bleeding episodes and repeat clinico-radiological assessment at end of follow up were recorded. When analyzed, statistically insignificant difference was found between the bleeding rates after the two prophylaxis regimes. There was a significant improvement between initial and final clinical and radiological scores in both the groups and no difference was recorded in between the groups. To conclude, twice weekly FVIII therapy is effective, easily administered prophylactic schedule to prevent long-term complications of hemophilia A.
血友病的低剂量因子 VIII 预防性治疗至今尚未得到很好的确立。本随机对照试验比较了两次与每周三次低剂量预防性因子 VIII 方案在儿童血友病 A 中的疗效,通过出血率和临床放射学评估进行评估。
将 33 名严重血友病 A(≤18 岁)患儿随机分为两组。基线评估包括详细病史、临床(HJHS 2.1 评分和 FISH 评分)和放射学检查(Pettersson 评分和超声评分)。第 1 组接受每周两次的因子 VIII 预防治疗,第 2 组接受每周三次的因子 VIII 预防治疗,两组的剂量均为 10 U/kg。所有参与者在接下来的 6 个月至 1 年内进行随访。记录急性出血发作和随访结束时重复临床放射学评估的数据。
我们分析了每周两次预防组的 14 名儿童和每周三次预防组的 16 名儿童。两组预防后的出血率差异无统计学意义,中位数每月出血率为 0.17,p 值为 0.79。两组内初始和最终临床和放射学评分之间的差异具有统计学意义。两组之间的临床和放射学评分无显著差异。
每周两次 FVIII 治疗是一种有效、易于管理的预防方案,可预防血友病 A 的长期并发症。
注:以上为译文,仅供参考。