Lee Christina S, Kim Jason S, Rodriguez Rosemarie, Krell Robert W
General Surgery, San Antonio Military Medical Center, San Antonio, USA.
Radiology, Brooke Army Medical Center, San Antonio, USA.
Cureus. 2022 Apr 23;14(4):e24422. doi: 10.7759/cureus.24422. eCollection 2022 Apr.
Inflammatory myofibroblastic tumors (IMTs) are rare mesenchymal neoplasms containing spindle cells and inflammatory components that can be locally aggressive. They have unclear biological behavior and may recur after resection. A 31-year-old woman presented with three months of cough, fatigue, weight loss, abdominal pain, anemia, and elevated inflammatory markers. CT showed a large well-circumscribed enhancing mass in the right colic mesentery. The patient underwent a laparoscopic right colectomy. Pathologic review showed fascicular spindle cells with admixed chronic inflammatory cells. Cells stained diffusely positive for SMA and anaplastic lymphoma kinase (ALK), diagnostic of an IMT. Post-operatively, the patient reported symptom resolution and had normalization of lab values. She remains disease-free at 20 months. IMT is rare in adults, accounting for 0.7%-1.0% of lung tumors. Up to 30% of patients present with elevated inflammatory markers. On imaging, IMTs are soft tissue masses with variable enhancement and fibrosis, often suspected to be malignant neoplasms. Up to 80% of IMTs are driven by altered tyrosine kinase signaling and half of IMTs express ALK, which may be treated in unresectable/recurrent cases using ALK-inhibitors. IMT may recur in 10%-15% of patients. The roles of adjuvant treatments are unclear given the rarity and unpredictable biological behavior. Long-term follow-up with regular radiologic and laboratory surveillance is recommended given possible local recurrence. IMTs are best managed in a multidisciplinary setting given their unpredictable nature. Surgery is the mainstay of IMT treatment with long-term control expected in >80% of adult patients.
炎性肌纤维母细胞瘤(IMTs)是一种罕见的间叶性肿瘤,由梭形细胞和炎症成分组成,具有局部侵袭性。其生物学行为尚不明确,切除后可能复发。一名31岁女性出现咳嗽、乏力、体重减轻、腹痛、贫血及炎症标志物升高3个月。CT显示右结肠系膜有一个边界清晰的巨大强化肿块。患者接受了腹腔镜右半结肠切除术。病理检查显示为束状梭形细胞,伴有混合性慢性炎症细胞。细胞对平滑肌肌动蛋白(SMA)和间变性淋巴瘤激酶(ALK)呈弥漫性阳性染色,确诊为IMT。术后,患者症状缓解,实验室检查值恢复正常。20个月来她一直无病生存。IMT在成人中罕见,占肺肿瘤的0.7%-1.0%。高达30%的患者炎症标志物升高。在影像学上,IMT是具有不同程度强化和纤维化的软组织肿块,常被怀疑为恶性肿瘤。高达80%的IMT由酪氨酸激酶信号改变驱动,一半的IMT表达ALK,在不可切除/复发病例中可用ALK抑制剂治疗。10%-15%的患者IMT可能复发。鉴于其罕见性和不可预测的生物学行为,辅助治疗的作用尚不清楚。鉴于可能的局部复发,建议进行定期影像学和实验室监测的长期随访。鉴于IMT性质不可预测,最好在多学科环境中进行管理。手术是IMT治疗的主要手段,预计>80%的成年患者可获得长期控制。