Hsu Chia-Chen, Wang Ying-Hsuan, Chen Yi-Yang, Chen Ying-Ju, Lu Chang-Hsien, Wu Yu-Ying, Yang Yao-Ren, Tsou Hsing-Yi, Li Chian-Pei, Huang Cih-En, Chen Chih-Cheng
Division of Hematology and Oncology, Department of Medicine, Chang Gung Memorial Hospital, Chiayi 61363, Taiwan.
College of Medicine, Chang Gung University, Tao-Yuan 33302, Taiwan.
Cancers (Basel). 2022 Jul 14;14(14):3435. doi: 10.3390/cancers14143435.
Patients with myeloproliferative neoplasms (MPNs) are characterized by systemic inflammation. With the indolent nature of the diseases, second cancers (SCs) have emerged as a challenging issue in afflicted patients. Epidemiological studies have confirmed the excessive risk of SCs in MPNs, but little is known about their molecular basis. To explore further, we used whole exome sequencing to explore the genetic changes in the granulocytes of 26 paired MPN patients with or without SC. We noticed that MPN−SC patients harbor genomic variants of distinct genes, among which a unique pattern of co-occurrence or mutual exclusiveness could be identified. We also found that mutated genes in MPN−SC samples were enriched in immune-related pathways and inflammatory networks, an observation further supported by their increased plasma levels of TGF-β and IL-23. Noteworthily, variants of KRT6A, a gene capable of mediating tumor-associate macrophage activity, were more commonly detected in MPN−SC patients. Analysis through OncodriveCLUST disclosed that KRT6A replaces JAK2V617F as the more prominent disease driver in MPN−SC, whereas a major mutation in this gene (KRT6A c.745T>C) in our patients is linked to human carcinoma and predicted to be pathogenic in COSMIC database. Overall, we demonstrate that inflammation could be indispensable in MPN−SC pathogenesis.
骨髓增殖性肿瘤(MPNs)患者具有全身炎症特征。鉴于这些疾病的惰性本质,第二原发癌(SCs)已成为困扰患者的一个具有挑战性的问题。流行病学研究已证实MPNs患者发生SCs的风险过高,但对其分子基础知之甚少。为了进一步探索,我们使用全外显子组测序来研究26例配对的有或无SCs的MPN患者粒细胞中的基因变化。我们注意到MPN-SC患者存在不同基因的基因组变异,其中可以识别出独特的共现或互斥模式。我们还发现,MPN-SC样本中的突变基因在免疫相关途径和炎症网络中富集,血浆中TGF-β和IL-23水平升高进一步支持了这一观察结果。值得注意的是,能够介导肿瘤相关巨噬细胞活性的基因KRT6A的变异在MPN-SC患者中更常见。通过OncodriveCLUST分析发现,KRT6A取代JAK2V617F成为MPN-SC中更突出的疾病驱动因素,而我们患者中该基因的一个主要突变(KRT6A c.745T>C)与人类癌症相关,并且在COSMIC数据库中预测具有致病性。总体而言,我们证明炎症在MPN-SC发病机制中可能不可或缺。