Department of Neurosurgery, Great Ormond Street Hospital, London, UK.
Department of Metabolic Medicine, Great Ormond Street Hospital, London, UK.
Adv Tech Stand Neurosurg. 2022;45:199-228. doi: 10.1007/978-3-030-99166-1_6.
Since its first description in 1994, convection-enhanced delivery (CED) has become a reliable method of administering drugs directly into the brain parenchyma. More predictable and effective than simple diffusion, CED bypasses the challenging boundary of the blood brain barrier, which has frustrated many attempts at delivering large molecules or polymers into the brain parenchyma. Although most of the clinical work with CED has been carried out on adults with incurable neoplasms, principally glioblastoma multiforme, an increasing number of studies have recognized its potential for paediatric applications, which now include treatment of currently incurable brain tumours such as diffuse intrinsic pontine glioma (DIPG), as well as metabolic and neurotransmitter diseases. The roadmap for the development of hardware and use of pharmacological agents in CED has been well-established, and some neurosurgical centres throughout the world have successfully undertaken clinical trials, admittedly mostly early phase, on the basis of in vitro, small animal and large animal pre-clinical foundations. However, the clinical efficacy of CED, although theoretically logical, has yet to be unequivocally demonstrated in a clinical trial; this applies particularly to neuro-oncology.This review aims to provide a broad description of the current knowledge of CED as applied to children. It reviews published studies of paediatric CED in the context of its wider history and developments and underlines the challenges related to the development of hardware, the selection of pharmacological agents, and gene therapy. It also reviews the difficulties related to the development of clinical trials involving CED and looks towards its potential disease-modifying opportunities in the future.
自 1994 年首次描述以来,对流增强输送(CED)已成为将药物直接输送到脑实质的可靠方法。与简单的扩散相比,CED 更具可预测性和有效性,它绕过了血脑屏障的挑战性边界,这使得许多向脑实质输送大分子或聚合物的尝试都失败了。尽管 CED 的大部分临床工作都是在患有绝症的成人身上进行的,主要是多形性胶质母细胞瘤,但越来越多的研究已经认识到其在儿科应用中的潜力,现在包括治疗目前无法治愈的脑瘤,如弥漫性内在脑桥胶质瘤(DIPG),以及代谢和神经递质疾病。CED 中硬件开发和药理学制剂使用的路线图已经建立,世界上一些神经外科中心已经成功地根据体外、小动物和大动物临床前基础进行了临床试验,尽管大多是早期阶段。然而,CED 的临床疗效,尽管在理论上是合理的,但尚未在临床试验中得到明确证明;这尤其适用于神经肿瘤学。本综述旨在广泛描述 CED 在儿科中的应用的现有知识。它回顾了发表的儿科 CED 研究,以了解其更广泛的历史和发展,并强调了与硬件开发、药理学制剂选择和基因治疗相关的挑战。它还回顾了与 CED 临床试验开发相关的困难,并展望了其未来潜在的疾病修饰机会。