Department of Pediatrics, Feinberg School of Medicine, Northwestern University, Chicago, Illinois, USA.
Pediatric Nephrology, Ann and Robert H. Lurie Children's Hospital of Chicago, Chicago, Illinois, USA.
JCI Insight. 2022 Nov 8;7(21):e160977. doi: 10.1172/jci.insight.160977.
We previously reported that Smad anchor for receptor activation (SARA) plays a critical role in maintaining epithelial cell phenotype. Here, we show that SARA suppressed myofibroblast precursor transdifferentiation in a mouse model of scleroderma. Mice overexpressing SARA specifically in PDGFR-β+ pericytes and pan-leukocytes (SARATg) developed significantly less skin fibrosis in response to bleomycin injection compared with wild-type littermates (SARAWT). Single-cell RNA-Seq analysis of skin PDGFR-β+ cells implicated pericyte subsets assuming myofibroblast characteristics under fibrotic stimuli, and SARA overexpression blocked the transition. In addition, a cluster that expresses molecules associated with Th2 cells and macrophage activation was enriched in SARAWT mice, but not in SARATg mice, after bleomycin treatment. Th2-specific Il-31 expression was increased in skin of the bleomycin-treated SARAWT mice and patients with scleroderma (or systemic sclerosis, SSc). Receptor-ligand analyses indicated that lymphocytes mediated pericyte transdifferentiation in SARAWT mice, while with SARA overexpression the myofibroblast activity of pericytes was suppressed. Together, these data suggest a potentially novel crosstalk between myofibroblast precursors and immune cells in the pathogenesis of SSc, in which SARA plays a critical role.
我们之前报道称,Smad 锚蛋白受体激活物(SARA)在维持上皮细胞表型方面起着关键作用。在这里,我们表明 SARA 抑制了硬皮病小鼠模型中的成肌纤维细胞前体转分化。与野生型同窝仔鼠(SARAWT)相比,特异性在 PDGFR-β+周细胞和全白细胞中过表达 SARA 的小鼠(SARATg)在博来霉素注射后皮肤纤维化明显减少。皮肤 PDGFR-β+细胞的单细胞 RNA-Seq 分析表明,在纤维化刺激下,周细胞亚群假定具有成肌纤维细胞特征,而 SARA 过表达则阻断了这种转化。此外,在博来霉素处理后,SARAWT 小鼠中富含表达与 Th2 细胞和巨噬细胞激活相关分子的簇,但 SARATg 小鼠中则没有。在博来霉素处理的 SARAWT 小鼠和硬皮病(或系统性硬化症,SSc)患者的皮肤中,Th2 特异性 Il-31 表达增加。受体-配体分析表明,淋巴细胞介导了 SARAWT 小鼠中周细胞的转分化,而 SARA 过表达则抑制了周细胞的成肌纤维细胞活性。总之,这些数据表明,在 SSc 的发病机制中,成肌纤维细胞前体和免疫细胞之间可能存在一种新的串扰,而 SARA 在其中起着关键作用。