Graduate School of Bioindustry, Tokyo University of Agriculture, Abashiri 099-2493, Japan.
Regenerative Medicine Project, Tokyo Metropolitan Institute of Medical Science, Tokyo 156-8506, Japan.
Int J Mol Sci. 2022 Oct 6;23(19):11855. doi: 10.3390/ijms231911855.
Fibroblast growth factor 5 (FGF5) is an important molecule required for the transition from anagen to catagen phase of the mammalian hair cycle. We previously reported that Syrian hamsters harboring a 1-bp deletion in the Fgf5 gene exhibit excessive hair growth in males. Herein, we generated Fgf5 mutant mice using genome editing via oviductal nucleic acid delivery (GONAD)/improved GONAD (i-GONAD), an in vivo genome editing system used to target early embryos present in the oviductal lumen, to study gender differences in hair length in mutant mice. The two lines (Fgf5go-malc), one with a 2-bp deletion (c.552_553del) and the other with a 1-bp insertion (c.552_553insA) in exon 3 of Fgf5, were successfully established. Each mutation was predicted to disrupt a part of the FGF domain through frameshift mutation (p.Glu184ValfsX128 or p.Glu184ArgfsX128). Fgf5go-malc1 mice had heterogeneously distributed longer hairs than wild-type mice (C57BL/6J). Notably, this change was more evident in males than in females (p < 0.0001). Immunohistochemical analysis revealed the presence of FGF5 protein in the dermal papilla and outer root sheath of the hair follicles from C57BL/6J and Fgf5go-malc1 mice. Histological analysis revealed that the prolonged anagen phase might be the cause of accelerated hair growth in Fgf5go-malc1 mice.
成纤维细胞生长因子 5(FGF5)是哺乳动物毛发周期从生长期向退行期转变所必需的重要分子。我们之前的研究表明,携带 Fgf5 基因 1 个碱基缺失的叙利亚仓鼠雄性表现出过度的毛发生长。在此,我们利用卵道核酸递送(GONAD)/改良 GONAD(i-GONAD)进行基因组编辑在体内靶向卵道腔内的早期胚胎,生成 Fgf5 突变小鼠,以研究突变小鼠毛发长度的性别差异。该系统用于研究突变小鼠毛发长度的性别差异。成功建立了两条 Fgf5 基因第 3 外显子发生 2 个碱基缺失(c.552_553del)和 1 个碱基插入(c.552_553insA)的突变系(Fgf5go-malc)。每个突变都预测通过移码突变破坏 FGF 结构域的一部分(p.Glu184ValfsX128 或 p.Glu184ArgfsX128)。Fgf5go-malc1 小鼠的毛发比野生型小鼠(C57BL/6J)分布不均且更长。值得注意的是,这种变化在雄性中比在雌性中更为明显(p < 0.0001)。免疫组织化学分析显示,C57BL/6J 和 Fgf5go-malc1 小鼠的毛囊真皮乳头和外根鞘中存在 FGF5 蛋白。组织学分析表明,生长期的延长可能是 Fgf5go-malc1 小鼠毛发生长加速的原因。