Figueiredo Ana, Pereira Teresa, Cabrera Rafael, Simões-Pereira Joana, Leite Valeriano
Endocrinology, Instituto Português de Oncologia de Lisboa Francisco Gentil, Lisboa, PRT.
Pathology, Instituto Português de Oncologia de Lisboa Francisco Gentil, Lisboa, PRT.
Cureus. 2023 Jan 6;15(1):e33446. doi: 10.7759/cureus.33446. eCollection 2023 Jan.
Hypercalcemia of malignancy (HM) is a common form of paraneoplastic syndrome associated with a poor prognosis of the disease. In solid tumors, HM occurs mainly due to the production of parathyroid hormone-related peptide (PTHrP). We present a case of a 60-year-old male with a 25 cm retroperitoneal liposarcoma diagnosed with severe hypercalcemia (16.8 mg/dL) by a preoperative blood sampling. Hypercalcemia workup showed suppressed parathyroid hormone (PTH), normal PTHrP, and high 1,25-dihydroxyvitamin D (1,25(OH)2D) serum levels. After surgery, hypercalcemia and calcitriol levels normalized. Immunohistochemical analysis of the tumor showed 1α-hydroxylase expression by tumor cells. To our knowledge, this is the first case of liposarcoma-associated hypercalcemia caused exclusively by the ectopic production of calcitriol. Despite being a rare cause of hypercalcemia, measuring 1,25(OH)2D should be considered in the workup of a patient with high serum calcium levels, suppressed PTH, and normal PTHrP.
恶性肿瘤高钙血症(HM)是一种常见的副肿瘤综合征,与疾病的不良预后相关。在实体瘤中,HM主要是由于甲状旁腺激素相关肽(PTHrP)的产生所致。我们报告一例60岁男性,患有25 cm的腹膜后脂肪肉瘤,术前血液检查诊断为严重高钙血症(16.8 mg/dL)。高钙血症检查显示甲状旁腺激素(PTH)受抑制、PTHrP正常以及血清1,25-二羟维生素D(1,25(OH)2D)水平升高。手术后,高钙血症和骨化三醇水平恢复正常。肿瘤的免疫组织化学分析显示肿瘤细胞表达1α-羟化酶。据我们所知,这是首例仅由骨化三醇异位产生引起的脂肪肉瘤相关性高钙血症。尽管高钙血症的这种病因罕见,但对于血清钙水平高、PTH受抑制且PTHrP正常的患者,在检查过程中应考虑检测1,25(OH)2D。