Department of Obstetrics, Mid Cheshire Hospitals NHS Foundation Trust, Crewe, UK
Department of Obstetrics, Mid Cheshire Hospitals NHS Foundation Trust, Crewe, UK.
BMJ Case Rep. 2023 Mar 8;16(3):e251653. doi: 10.1136/bcr-2022-251653.
Gastrointestinal bleeding that originates in the small intestine is often difficult to diagnose. Bleeding from a small intestinal arteriovenous malformation (AVM) is rare, with congenital AVMs more commonly located in the rectum or sigmoid. There is a relative paucity of cases reported in the literature. In the gastrointestinal tract, it can cause acute and chronic bleeding, which can be fatal. Although the incidence of small bowel AVMs is quite low, such lesions can be identified as the bleeding source in patients with obscure gastrointestinal bleeding (OGIB) harbouring severe, transfusion-dependent anaemia. It can be exceedingly difficult to localise and diagnose gastrointestinal tract bleeding, particularly in cases of occult small bowel AVMs. CT angiography and capsule endoscopy can help to establish the diagnosis. Laparoscopy is an appropriate and beneficial treatment modality for small bowel resection. The authors present the case of a primigravida woman in her late 20s diagnosed with a symptomatic transfusion-dependent anaemia during her pregnancy. She developed OGIB and despite no history of chronic liver disease became encephalopathic. Due to her physical deterioration and uncertain diagnosis, her caesarean section was performed at 36+6 weeks to expedite investigations and treatment. She was diagnosed with a jejunal AVM and underwent coiled embolisation of her superior mesenteric artery. She became haemodynamically unstable and underwent a laparotomy and small bowel resection. A full non-invasive liver screen was negative, however, her MRI liver described multiple focal nodular hyperplasia (FNH) lesions raising the possibility of FNH syndrome in the context of a previous AVM malformation. A prompt stepwise, multimodality diagnostic approach is required to prevent patient morbidity and mortality.
起源于小肠的胃肠道出血通常难以诊断。小肠动静脉畸形(AVM)出血很少见,先天性 AVM 更常见于直肠或乙状结肠。文献中报道的病例相对较少。在胃肠道中,它可引起急性和慢性出血,这可能是致命的。虽然小肠 AVM 的发病率相当低,但在患有严重、依赖输血贫血的不明原因胃肠道出血(OGIB)患者中,这些病变可能被确定为出血源。定位和诊断胃肠道出血非常困难,尤其是在隐匿性小肠 AVM 的情况下。CT 血管造影和胶囊内镜有助于明确诊断。腹腔镜检查是一种合适且有益的小肠切除术治疗方式。作者介绍了一位 20 多岁的初产妇的病例,她在怀孕期间被诊断为症状性依赖输血的贫血。她出现了 OGIB,尽管没有慢性肝病病史,但出现了脑病。由于她的身体恶化和不确定的诊断,她在 36+6 周时进行了剖宫产,以加快检查和治疗。她被诊断为空肠 AVM,并接受了肠系膜上动脉的线圈栓塞治疗。她出现血流动力学不稳定,并进行了剖腹手术和小肠切除术。全面的非侵入性肝脏检查为阴性,但她的 MRI 肝脏描述了多个局灶性结节性增生(FNH)病变,这增加了先前 AVM 畸形背景下 FNH 综合征的可能性。需要进行快速、逐步的多模式诊断方法,以防止患者出现发病率和死亡率。