Basic and Clinical Immunology Service, Department of Pathology, Faculty of Medicine, University of Porto, Porto, Portugal.
Serviço de Imunoalergologia, São João University Hospital Center, Porto, Portugal.
Eur Ann Allergy Clin Immunol. 2023 Jul;55(4):152-160. doi: 10.23822/EurAnnACI.1764-1489.288. Epub 2023 Mar 16.
Hereditary α-tryptasemia (HαT) is a common autosomal dominant genetic trait with variable penetrance associated with increased serum baseline tryptase (SBT) levels. Clinical manifestations may range from an absence of symptoms to overtly severe and recurrent anaphylaxis. Symptoms have been claimed to result from excessive activation of EGF-like module-containing mucin-like hormone receptor-like 2 (EMR2) and protease-activated receptor 2 (PAR-2) receptors by α/β-tryptase heterotetramers. Herein, we aimed to review the evidence on whether HαT can be considered a hereditary risk factor or a modifying factor for anaphylaxis.Increased SBT levels have been linked to an increased risk of anaphylaxis. Likewise, recent studies have shown that HαT might be associated with a higher risk of developing anaphylaxis and more severe anaphylaxis. The same has also been shown for patients with clonal mast cell disorders, in whom the co-existence of HαT might lead to a greater propensity for severe, potentially life-threatening anaphylaxis. However, studies leading to such conclusions are generally limited in sample size, while other studies have shown opposing results. As such, further studies investigating the potential association of HαT with anaphylaxis caused by different triggers, and different severity grades, in both patients with clonal mast cell activation syndromes and the general population are still needed.
遗传性 α-胰蛋白酶血症 (HαT) 是一种常见的常染色体显性遗传特征,具有可变的外显率,与血清基础胰蛋白酶 (SBT) 水平升高有关。临床表现范围从无症状到明显严重和复发性过敏反应。据称,症状是由 α/β-胰蛋白酶异四聚体过度激活表皮生长因子样模块包含的粘蛋白样激素受体样 2 (EMR2) 和蛋白酶激活受体 2 (PAR-2) 受体引起的。在此,我们旨在回顾关于 HαT 是否可以被视为过敏反应的遗传风险因素或修饰因素的证据。SBT 水平升高与过敏反应风险增加有关。同样,最近的研究表明,HαT 可能与过敏反应风险增加和更严重的过敏反应相关。克隆肥大细胞疾病患者也是如此,其中 HαT 的共存可能导致更严重、潜在威胁生命的过敏反应的倾向更大。然而,导致此类结论的研究通常样本量有限,而其他研究则显示出相反的结果。因此,仍需要进一步研究 HαT 与克隆肥大细胞激活综合征患者和普通人群中不同触发因素和不同严重程度的过敏反应之间的潜在关联。