Mukhopadhyay Anirban, Deshpande Smita N, Bhatia Triptish, Thelma B K
Department of Genetics, University of Delhi South Campus, Benito Juarez Marg, New Delhi, 110021, India.
Department of Psychiatry, Postgraduate Institute of Medical Education and Research-Dr. Ram Manohar Lohia Hospital, New Delhi, India.
Eur Arch Psychiatry Clin Neurosci. 2023 Dec;273(8):1677-1691. doi: 10.1007/s00406-023-01596-9. Epub 2023 Apr 3.
Genetic etiology of schizophrenia is poorly understood despite large genome-wide association data. Long non-coding RNAs (lncRNAs) with a probable regulatory role are emerging as important players in neuro-psychiatric disorders including schizophrenia. Prioritising important lncRNAs and analyses of their holistic interaction with their target genes may provide insights into disease biology/etiology. Of the 3843 lncRNA SNPs reported in schizophrenia GWASs extracted using lincSNP 2.0, we prioritised n = 247 based on association strength, minor allele frequency and regulatory potential and mapped them to lncRNAs. lncRNAs were then prioritised based on their expression in brain using lncRBase, epigenetic role using 3D SNP and functional relevance to schizophrenia etiology. 18 SNPs were finally tested for association with schizophrenia (n = 930) and its endophenotypes-tardive dyskinesia (n = 176) and cognition (n = 565) using a case-control approach. Associated SNPs were characterised by ChIP seq, eQTL, and transcription factor binding site (TFBS) data using FeatSNP. Of the eight SNPs significantly associated, rs2072806 in lncRNA hsaLB_IO39983 with regulatory effect on BTN3A2 was associated with schizophrenia (p = 0.006); rs2710323 in hsaLB_IO_2331 with role in dysregulation of ITIH1 with tardive dyskinesia (p < 0.05); and four SNPs with significant cognition score reduction (p < 0.05) in cases. Two of these with two additional variants in eQTL were observed among controls (p < 0.05), acting likely as enhancer SNPs and/or altering TFBS of eQTL mapped downstream genes. This study highlights important lncRNAs in schizophrenia and provides a proof of concept of novel interactions of lncRNAs with protein-coding genes to elicit alterations in immune/inflammatory pathways of schizophrenia.
尽管有大量全基因组关联数据,但精神分裂症的遗传病因仍知之甚少。具有潜在调控作用的长链非编码RNA(lncRNA)正在成为包括精神分裂症在内的神经精神疾病的重要参与者。对重要的lncRNA进行优先级排序,并分析它们与靶基因的整体相互作用,可能有助于深入了解疾病生物学/病因。在使用lincSNP 2.0从精神分裂症全基因组关联研究(GWAS)中报告的3843个lncRNA单核苷酸多态性(SNP)中,我们根据关联强度、次要等位基因频率和调控潜力对n = 247个SNP进行了优先级排序,并将它们映射到lncRNA上。然后,使用lncRBase根据lncRNA在大脑中的表达、使用3D SNP根据表观遗传作用以及与精神分裂症病因的功能相关性对lncRNA进行优先级排序。最后,使用病例对照方法对18个SNP与精神分裂症(n = 930)及其内表型——迟发性运动障碍(n = 176)和认知(n = 565)进行关联测试。使用FeatSNP通过染色质免疫沉淀测序(ChIP seq)、表达数量性状基因座(eQTL)和转录因子结合位点(TFBS)数据对相关SNP进行特征分析。在8个显著相关的SNP中,lncRNA hsaLB_IO39983中对BTN3A2具有调控作用的rs2072806与精神分裂症相关(p = 0.006);hsaLB_IO_2331中的rs2710323与迟发性运动障碍中ITIH1的失调有关(p < 0.05);在病例中有4个SNP导致认知评分显著降低(p < 0.05)。在对照中观察到其中两个SNP与eQTL中的另外两个变体相关(p < 0.05),它们可能作为增强子SNP和/或改变eQTL定位的下游基因的TFBS。这项研究突出了精神分裂症中重要的lncRNA,并提供了lncRNA与蛋白质编码基因新相互作用以引发精神分裂症免疫/炎症途径改变的概念验证。