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"Embryonic-type Neuroectodermal Tumor" Should Replace "Primitive Neuroectodermal Tumor" of the Testis and Gynecologic Tract: A Rationale for New Nomenclature.“胚胎型神经外胚层肿瘤”应取代睾丸和生殖道的“原始神经外胚层肿瘤”:新命名的依据
Am J Surg Pathol. 2021 Oct 1;45(10):1299-1302. doi: 10.1097/PAS.0000000000001703.
2
Obesity and cancer risk: Emerging biological mechanisms and perspectives.肥胖与癌症风险:新兴的生物学机制与展望。
Metabolism. 2019 Mar;92:121-135. doi: 10.1016/j.metabol.2018.11.001. Epub 2018 Nov 13.
3
Proprotein convertase 1/3 inhibited macrophages: A novel therapeutic based on drone macrophages.前蛋白转化酶1/3抑制巨噬细胞:一种基于无人机巨噬细胞的新型疗法。
EuPA Open Proteom. 2016 Mar 5;11:20-22. doi: 10.1016/j.euprot.2016.03.003. eCollection 2016 Jun.
4
Long-Term Follow-up of a Case with Proprotein Convertase 1/3 Deficiency: Transient Diabetes Mellitus with Intervening Diabetic Ketoacidosis During Growth Hormone Therapy.前蛋白转化酶1/3缺乏症一例的长期随访:生长激素治疗期间出现短暂性糖尿病并伴有中间型糖尿病酮症酸中毒
J Clin Res Pediatr Endocrinol. 2017 Sep 1;9(3):283-287. doi: 10.4274/jcrpe.3986. Epub 2017 Jun 7.
5
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6
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Br J Haematol. 2017 Feb;176(4):539-552. doi: 10.1111/bjh.14461. Epub 2016 Dec 16.
7
PCSK1 Mutations and Human Endocrinopathies: From Obesity to Gastrointestinal Disorders.PCSK1 突变与人类内分泌疾病:从肥胖到胃肠道疾病。
Endocr Rev. 2016 Aug;37(4):347-71. doi: 10.1210/er.2015-1117. Epub 2016 May 17.
8
Molecular Consequences of Proprotein Convertase 1/3 (PC1/3) Inhibition in Macrophages for Application to Cancer Immunotherapy: A Proteomic Study.前蛋白转化酶1/3(PC1/3)抑制巨噬细胞对癌症免疫治疗的分子影响:一项蛋白质组学研究
Mol Cell Proteomics. 2015 Nov;14(11):2857-77. doi: 10.1074/mcp.M115.052480. Epub 2015 Sep 1.
9
Ewing sarcoma/peripheral primitive neuroectodermal tumor and related tumors.尤因肉瘤/外周原始神经外胚层肿瘤及相关肿瘤
Pediatr Dev Pathol. 2012;15(1 Suppl):108-26. doi: 10.2350/11-08-1078-PB.1.
10
Clinical features and outcomes in patients with extraskeletal Ewing sarcoma.骨外尤文肉瘤患者的临床特征和转归。
Cancer. 2011 Jul 1;117(13):3027-32. doi: 10.1002/cncr.25840. Epub 2011 Jan 10.

伴有盆腔尤因肉瘤的前蛋白转化酶1/3缺乏症

PROPROTEIN CONVERTASE 1/3 DEFICIENCY WITH PELVIC EWING SARCOMA.

作者信息

Oral H, Guven D C, Özdemir D Ateş, Usubütün A, Gonc N, Arik Z

机构信息

Department of Internal Medicine, Hacettepe University Faculty of Medicine, Ankara, Turkey.

Department of Internal Medicine, Division of Oncology, Hacettepe University Faculty of Medicine, Ankara, Turkey.

出版信息

Acta Endocrinol (Buchar). 2022 Oct-Dec;18(4):508-511. doi: 10.4183/aeb.2022.508.

DOI:10.4183/aeb.2022.508
PMID:37152885
原文链接:https://pmc.ncbi.nlm.nih.gov/articles/PMC10162823/
Abstract

Proprotein convertase 1/3 (PC 1/3) deficiency is a rare, autosomal recessive disorder caused by mutations in the PCSK1 gene. The disease is characterized by early-onset chronic diarrhea/malabsorption, followed by severe obesity and hormonal deficiencies such as hypocortisolism, hypothyroidism, diabetes insipidus, hypogonadism, growth deficiency, and diabetes mellitus. Ewing's sarcoma is a rare tumor, usually of small dimensions of neuroectodermal origin that is difficult to distinguish pathologically from a primitive neuroectodermal tumor. A 22-year-old female patient with PC 1/3 deficiency was admitted to our clinic with recurrent urinary tract infections. Magnetic resonance imaging (MRI) revealed an 11x12 cm pelvic mass displacing the uterus. A core-needle biopsy was performed on the pelvic mass. As a result of the pathological evaluation, ıt was diagnosed with pelvic Ewing's sarcoma. The patient was started on the VAC-IE chemotherapy protocol. We report a case of pelvic Ewing's sarcoma in a patient with PC 1/3 deficiency. Further research is needed to assess malignancy risk in metabolic disorders including very rare disorders like PC 1/3 deficiency.

摘要

前蛋白转化酶1/3(PC 1/3)缺乏症是一种罕见的常染色体隐性疾病,由PCSK1基因突变引起。该疾病的特征是早发性慢性腹泻/吸收不良,随后出现严重肥胖和激素缺乏,如皮质醇减少症、甲状腺功能减退、尿崩症、性腺功能减退、生长发育迟缓以及糖尿病。尤因肉瘤是一种罕见肿瘤,通常体积较小,起源于神经外胚层,在病理上难以与原始神经外胚层肿瘤区分开来。一名患有PC 1/3缺乏症的22岁女性患者因反复尿路感染入住我院。磁共振成像(MRI)显示盆腔有一个11×12厘米的肿块,使子宫移位。对盆腔肿块进行了粗针活检。病理评估结果显示,该患者被诊断为盆腔尤因肉瘤。患者开始接受VAC-IE化疗方案治疗。我们报告了一例患有PC 1/3缺乏症的患者发生盆腔尤因肉瘤的病例。需要进一步研究来评估包括PC 1/3缺乏症等非常罕见疾病在内的代谢紊乱中的恶性肿瘤风险。