Department of Pharmacology and Toxicology, College of Pharmacy, University of Utah, Salt Lake City, UT, USA.
Department of Psychiatry, School of Medicine, Yale University, New Haven, CT, USA.
Neuropsychopharmacology. 2023 Aug;48(9):1288-1299. doi: 10.1038/s41386-023-01603-6. Epub 2023 May 17.
Ample evidence suggests that acute stress can worsen symptom severity in Tourette syndrome (TS); however, the neurobiological underpinnings of this phenomenon remain poorly understood. We previously showed that acute stress exacerbates tic-like and other TS-associated responses via the neurosteroid allopregnanolone (AP) in an animal model of repetitive behavioral pathology. To verify the relevance of this mechanism to tic pathophysiology, here we tested the effects of AP in a mouse model recapitulating the partial depletion of dorsolateral cholinergic interneurons (CINs) seen in post-mortem studies of TS. Mice underwent targeted depletion of striatal CINs during adolescence and were tested in young adulthood. Compared with controls, partially CIN-depleted male mice exhibited several TS-relevant abnormalities, including deficient prepulse inhibition (PPI) and increased grooming stereotypies after a 30-min session of spatial confinement - a mild acute stressor that increases AP levels in the prefrontal cortex (PFC). These effects were not seen in females. Systemic and intra-PFC AP administration dose-dependently worsened grooming stereotypies and PPI deficits in partially CIN-depleted males. Conversely, both AP synthesis inhibition and pharmacological antagonism reduced the effects of stress. These results further suggest that AP in the PFC mediates the adverse effects of stress on the severity of tics and other TS-related manifestations. Future studies will be necessary to confirm these mechanisms in patients and define the circuitry responsible for the effects of AP on tics.
大量证据表明,急性应激会加重抽动秽语综合征(TS)的症状严重程度;然而,这一现象的神经生物学基础仍知之甚少。我们之前的研究表明,在重复性行为病理学的动物模型中,通过神经甾体别孕烯醇酮(AP),急性应激会加剧抽搐样和其他与 TS 相关的反应。为了验证该机制与抽搐病理生理学的相关性,我们在此在模拟 TS 死后研究中观察到的背外侧胆碱能中间神经元(CIN)部分耗竭的小鼠模型中测试了 AP 的作用。在青春期期间,小鼠经历了纹状体 CIN 的靶向耗竭,并在成年早期进行了测试。与对照组相比,部分 CIN 耗竭的雄性小鼠表现出几种与 TS 相关的异常,包括前脉冲抑制(PPI)缺陷和在 30 分钟的空间限制后增加的修饰行为 - 一种轻度的急性应激源,可增加前额叶皮质(PFC)中的 AP 水平。这些影响在雌性中并未出现。系统和 PFC 内的 AP 给药剂量依赖性地加重了部分 CIN 耗竭雄性小鼠的修饰行为和 PPI 缺陷。相反,AP 合成抑制和药理学拮抗都降低了应激的影响。这些结果进一步表明,PFC 中的 AP 介导了应激对抽搐严重程度和其他 TS 相关表现的不利影响。未来的研究将有必要在患者中证实这些机制,并确定 AP 对抽搐影响的相关电路。