Ise Koki, Tanei Zen-Ichi, Oda Yoshitaka, Tanikawa Satoshi, Sugino Hirokazu, Ishida Yusuke, Tsuda Masumi, Gotoda Yuko, Nishiwaki Kunihiko, Yanai Hiroyuki, Hasegawa Tadashi, Nagashima Kazuo, Tanaka Shinya
Int J Gynecol Pathol. 2024 Jan 1;43(1):41-46. doi: 10.1097/PGP.0000000000000949. Epub 2023 Jun 14.
Uterine tumor resembling ovarian sex cord tumor (UTROSCT) is a rare tumor with low malignant potential that commonly occurs in middle age. Although more than 100 cases have been reported to date, myxoid morphology is not well documented. Here, we present a 75-yr-old woman with abnormal vaginal bleeding, with an 8-cm mass in the uterine corpus detected by irregular, high-intensity signaling on T2-weighted imaging. The uterine mass had a glistening mucinous appearance on gross examination. Microscopically, most of the tumor cells were floating in the myxoid stroma. The tumor cells formed clusters or nests with abundant cytoplasm, while some exhibited trabecular or rhabdoid appearances. Immunohistochemically, tumor cells were positive for pancytokeratin (AE1/AE3), α-smooth muscle actin, CD10, progesterone receptor, and some sex cord markers such as calretinin, inhibin, CD56, steroidogenic factor-1. Electron microscopy demonstrated epithelial and sex cord differentiation. This tumor was negative for JAZF1-JJAZ1 fusion gene that is frequently found in low-grade endometrial stromal sarcoma. Fusion genes related to UTROSCT, including NCOA2/3 , were not detected by reverse transcription polymerase chain reaction. The present case suggests that UTROSCT should be included in the differential diagnosis of myxoid uterine tumors.
子宫肿瘤样卵巢性索肿瘤(UTROSCT)是一种恶性潜能较低的罕见肿瘤,常见于中年。尽管迄今为止已报道了100多例病例,但黏液样形态的记录并不充分。在此,我们报告一名75岁有异常阴道出血的女性,通过T2加权成像上不规则的高强度信号检测到子宫体有一个8厘米的肿块。大体检查时,子宫肿块有光泽的黏液样外观。显微镜下,大多数肿瘤细胞漂浮在黏液样基质中。肿瘤细胞形成具有丰富细胞质的簇或巢,而有些则表现出小梁状或横纹肌样外观。免疫组化显示,肿瘤细胞对全细胞角蛋白(AE1/AE3)、α平滑肌肌动蛋白、CD10、孕激素受体以及一些性索标记物如钙视网膜蛋白、抑制素、CD56、类固醇生成因子-1呈阳性。电子显微镜显示有上皮和性索分化。该肿瘤的JAZF1-JJAZ1融合基因阴性,该融合基因在低级别子宫内膜间质肉瘤中常见。通过逆转录聚合酶链反应未检测到与UTROSCT相关的融合基因,包括NCOA2/3。本病例提示UTROSCT应纳入黏液样子宫肿瘤的鉴别诊断。