Mamedova E O, Lisina D V, Belaya Zh E
Endocrinology Research Centre.
Probl Endokrinol (Mosk). 2023 May 11;69(2):24-30. doi: 10.14341/probl13196.
Functioning pituitary adenomas and pheochromocytomas/paragangliomas are rare in the general population. Pituitary adenomas occur in the familial setting in approximately 5% of cases, whereas pheochromocytomas/paragangliomas can be hereditary in 30-40% of cases. Hereditary syndromes associated with pituitary adenomas include multiple endocrine neoplasia types 1 and 4, familial isolated pituitary adenomas, and Carney complex. Hereditary syndromes associated with pheochromocytomas/paragangliomas and genes, mutations in which predispose to their development, are more numerous. The first clinical descriptions of the co-occurrence of pituitary adenoma and pheochromocytoma/paraganglioma in one patient date back to the mid 20th century, however delineating such a co-occurrence into a particular syndrome («3PAs» (pituitary adenoma, pheochromocytoma, paraganglioma)) was suggested only in 2015. To date, approximately 100 cases of such a co-occurrence have been described in the literature. Mutations in genes encoding subunits of succinate dehydrogenase complex II (SDHx) are revealed in the majority of cases, much less common are mutations in MAX, MEN1 and some other genes. This review summarizes the current information on the «3PAs» syndrome.
功能性垂体腺瘤和嗜铬细胞瘤/副神经节瘤在普通人群中较为罕见。垂体腺瘤约5%发生于家族性病例中,而嗜铬细胞瘤/副神经节瘤30 - 40%可能具有遗传性。与垂体腺瘤相关的遗传性综合征包括1型和4型多发性内分泌腺瘤病、家族性孤立性垂体腺瘤以及卡尼综合征。与嗜铬细胞瘤/副神经节瘤相关的遗传性综合征以及其发生发展与之相关的基因突变更多。关于垂体腺瘤和嗜铬细胞瘤/副神经节瘤在同一患者中共存的首次临床描述可追溯到20世纪中叶,然而直到2015年才有人提出将这种共存情况界定为一种特殊综合征(“3PAs”(垂体腺瘤、嗜铬细胞瘤、副神经节瘤))。迄今为止,文献中已描述了约100例这种共存情况。大多数病例中发现了编码琥珀酸脱氢酶复合物II(SDHx)亚基的基因突变,而MAX、MEN1和其他一些基因的突变则较为少见。本综述总结了关于“3PAs”综合征的当前信息。