Drake Danielle M, Zhen Danlin, Kerrebijn Isabel, Or Benjamin, Gao Sophie, Afsharian Kian, Tran Jason, Bhatia Shama, Cheng Ashley, Wells Peter G
Department of Pharmaceutical Sciences, Faculty of Pharmacy, University of Toronto, Toronto, Ontario, Canada; Centre for Pharmaceutical Oncology, Faculty of Pharmacy, University of Toronto, Toronto, Ontario, Canada.
Department of Pharmaceutical Sciences, Faculty of Pharmacy, University of Toronto, Toronto, Ontario, Canada.
Free Radic Biol Med. 2023 Nov 1;208:272-284. doi: 10.1016/j.freeradbiomed.2023.08.006. Epub 2023 Aug 3.
The breast cancer 1 (Brca1) susceptibility gene regulates the repair of reactive oxygen species (ROS)-mediated DNA damage, which is implicated in neurodevelopmental disorders. Alcohol (ethanol, EtOH) exposure during pregnancy causes fetal alcohol spectrum disorders (FASD), including abnormal brain function, associated with enhanced ROS-initiated DNA damage. Herein, oxidative DNA damage in fetal brains and neurodevelopmental disorders were enhanced in saline-exposed +/- vs. +/+ Brca1 littermates. A single EtOH exposure during gestation further enhanced oxidative DNA damage, altered the expression of developmental/DNA damage response genes in fetal brains, and resulted in neurodevelopmental disorders, all of which were BRCA1-dependent. Pretreatment with the ROS inhibitor phenylbutylnitrone (PBN) blocked DNA damage and some neurodevelopmental disorders in both saline- and EtOH-exposed progeny, corroborating a ROS-dependent mechanism. Fetal BRCA1 protects against altered gene expression and neurodevelopmental disorders caused by both physiological and EtOH-enhanced levels of ROS formation. BRCA1 deficiencies may enhance the risk for FASD.
乳腺癌1(Brca1)易感基因调控活性氧(ROS)介导的DNA损伤修复,而这与神经发育障碍有关。孕期酒精(乙醇,EtOH)暴露会导致胎儿酒精谱系障碍(FASD),包括脑功能异常,这与ROS引发的DNA损伤增强有关。在此,与野生型Brca1同窝幼崽相比,生理盐水处理的Brca1杂合子同窝幼崽的胎儿脑内氧化DNA损伤和神经发育障碍有所增强。孕期单次EtOH暴露进一步增强了氧化DNA损伤,改变了胎儿脑内发育/DNA损伤反应基因的表达,并导致神经发育障碍,所有这些均依赖于BRCA1。用ROS抑制剂苯基丁基硝酮(PBN)预处理可阻断生理盐水和EtOH暴露后代的DNA损伤及部分神经发育障碍,证实了一种依赖于ROS的机制。胎儿BRCA1可预防由生理水平及EtOH增强的ROS生成水平所导致的基因表达改变和神经发育障碍。BRCA1缺陷可能会增加FASD的风险。