Nigrovic Peter A, Wang Qiang, Kim Taehyeung, Martinez-Bonet Marta, Aguiar Vitor R C, Sim Sangwan, Cui Jing, Sparks Jeffrey A, Chen Xiaoting, Todd Marc, Wauford Brian, Marion Miranda C, Langefeld Carl D, Weirauch Matthew T, Gutierrez-Arcelus Maria
bioRxiv. 2024 Apr 12:2023.08.16.553538. doi: 10.1101/2023.08.16.553538.
Genome-wide association studies implicate multiple loci in risk for systemic lupus erythematosus (SLE), but few contain exonic variants, rendering systematic identification of non-coding variants essential to decoding SLE genetics. We utilized SNP-seq and bioinformatic enrichment to interrogate 2180 single-nucleotide polymorphisms (SNPs) from 87 SLE risk loci for potential binding of transcription factors and related proteins from B cells. 52 SNPs that passed initial screening were tested by electrophoretic mobility shift and luciferase reporter assays. To validate the approach, we studied rs2297550 in detail, finding that the risk allele enhanced binding to the transcription factor Ikaros (IKZF1), thereby modulating expression of IKBKE. Correspondingly, primary cells from genotyped healthy donors bearing the risk allele expressed higher levels of the interferon / NF-κB regulator IKKϵ. Together, these findings define a set of likely functional non-coding lupus risk variants and identify a new regulatory pathway involving rs2297550, Ikaros, and IKKϵ implicated by human genetics in risk for SLE.
全基因组关联研究表明多个基因座与系统性红斑狼疮(SLE)风险相关,但其中很少包含外显子变异,因此系统鉴定非编码变异对于解读SLE遗传学至关重要。我们利用SNP测序和生物信息学富集技术,对来自87个SLE风险基因座的2180个单核苷酸多态性(SNP)进行检测,以探究B细胞中转录因子和相关蛋白的潜在结合情况。通过电泳迁移率变动分析和荧光素酶报告基因检测,对52个通过初步筛选的SNP进行了测试。为了验证该方法,我们对rs2297550进行了详细研究,发现风险等位基因增强了与转录因子Ikaros(IKZF1)的结合,从而调节IKBKE的表达。相应地,携带风险等位基因的基因分型健康供体的原代细胞表达了更高水平的干扰素/NF-κB调节因子IKKε。这些发现共同定义了一组可能具有功能的非编码狼疮风险变异,并确定了一条涉及rs2297550、Ikaros和IKKε的新调控途径,该途径在人类遗传学中与SLE风险相关。