Hoots W K, Huntington D, Devine D, Schmidt C, Bracey A
Am J Pediatr Hematol Oncol. 1986 Fall;8(3):225-30. doi: 10.1097/00043426-198623000-00009.
We describe acute therapy for a 13-year-old female from Panama with chronic idiopathic thrombocytopenia purpura (ITP) refractory to steroids, splenectomy, vinca alkaloids, and azathioprine. She presented with neurologic deterioration from a posterior fossa intracranial hemorrhage (ICH). This followed a 3-month history of severe dysfunctional uterine bleeding, progressive from menarche, which had required multiple red cell transfusions. Steroid and vinblastine therapy and transfusion of 40 U of platelets failed to increase the platelet count above 10,000/microliter. Development of a second larger ICH (frontal) produced morbid increase in intracranial pressure that necessitated neurosurgical decompression. Plasma exchange and colloid repletion with intravenous gamma globulin (1 g/kg) and an infusion of 20 U of platelets resulted in a transient rise in platelet count to 160,000/microliter, permitting surgery without bleeding. Danazol (800 mg/day) and conjugated estrogen (Premarin 25 mg/day) were begun to control the uterine bleeding. Intensive plasma exchange and i.v. IgG infusions were continued daily for 24 days, then twice weekly for several weeks. Platelet-bound IgG decreased almost 500% over the first 10 days of therapy, and platelets increased dramatically to 600,000/microliter after 3 weeks of therapy. The patient has remained amenorrheic with a normal platelet count for more than 24 months on daily danazol therapy and monthly infusions of i.v. IgG (0.4 g/kg/dose).
我们描述了一名来自巴拿马的13岁女性慢性特发性血小板减少性紫癜(ITP)患者的急性治疗情况,该患者对类固醇、脾切除术、长春花生物碱和硫唑嘌呤均无反应。她因后颅窝颅内出血(ICH)出现神经功能恶化。在此之前,她有3个月严重功能失调性子宫出血的病史,自初潮起病情逐渐加重,曾多次输注红细胞。类固醇和长春碱治疗以及输注40单位血小板未能使血小板计数升至10,000/微升以上。第二次更大的ICH(额叶)导致颅内压病态升高,需要进行神经外科减压。血浆置换以及静脉注射γ球蛋白(1 g/kg)和输注20单位血小板使血小板计数短暂升至160,000/微升,从而能够在无出血的情况下进行手术。开始使用达那唑(800 mg/天)和结合雌激素(Premarin 25 mg/天)来控制子宫出血。每天持续进行强化血浆置换和静脉注射免疫球蛋白,共24天,之后每周两次,持续数周。在治疗的前10天,血小板结合的免疫球蛋白下降了近500%,治疗3周后血小板急剧增加至600,000/微升。在每日服用达那唑以及每月静脉注射免疫球蛋白(0.4 g/kg/剂量)的情况下,患者停经且血小板计数正常已超过24个月。