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石骨症-佝偻病:两种矛盾的表现——一个统一的诊断。

Osteopetrorickets: two contradictory patterns-one unifying diagnosis.

机构信息

Memorial Sloan Kettering Cancer Center, Department of Radiology, New York, NY, 10065, USA.

Memorial Sloan Kettering Cancer Center, Department of Pediatrics, New York, NY, USA.

出版信息

Skeletal Radiol. 2024 Apr;53(4):817-820. doi: 10.1007/s00256-023-04443-z. Epub 2023 Sep 6.

Abstract

A 5-month-old infant with bone findings on x-ray presented an apparent contradiction including findings of both diffusely dense bones and rickets in the context of a history and laboratory investigation that suggested leukemia. Next generation gene panel sequencing revealed a TCIRG1 mutation which is consistent with autosomal recessive osteopetrosis. The paradoxical x-ray findings underscore a recently elucidated mechanism for the pathogenesis of a TCIRG mutation. This case highlights the importance of recognizing this radiographic, seeming contradictory, association in the context of a confusing clinical presentation. Failure to recognize this pattern promptly may lead to a delay in diagnosis, thus potentially permanent organ failure.

摘要

一名 5 个月大的婴儿,其 X 光片显示骨骼异常,表现出明显的矛盾,既有弥漫性骨密度增高,又有佝偻病的表现,结合病史和实验室检查结果提示白血病。下一代基因面板测序显示 TCIRG1 基因突变,符合常染色体隐性骨硬化症。矛盾的 X 光片表现强调了 TCIRG 基因突变发病机制的一个新阐明的机制。该病例突出了在复杂临床表现的背景下,认识到这种影像学上看似矛盾的关联的重要性。如果不能及时识别这种模式,可能会导致诊断延迟,从而可能导致永久性器官衰竭。

相似文献

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Infantile malignant osteopetrosis.婴儿恶性骨硬化症
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Osteopetrorickets: case report.骨质石化性佝偻病:病例报告
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本文引用的文献

1
Imaging in osteopetrosis.成骨不全症的影像学表现。
Bone. 2022 Dec;165:116560. doi: 10.1016/j.bone.2022.116560. Epub 2022 Sep 15.
4
How we approach malignant infantile osteopetrosis.我们如何治疗婴儿恶性成骨性骨硬化症。
Pediatr Blood Cancer. 2021 Mar;68(3):e28841. doi: 10.1002/pbc.28841. Epub 2020 Dec 12.
8
Malignant infantile osteopetrosis: case report with review of literature.恶性婴儿骨硬化症:病例报告并文献复习
Pan Afr Med J. 2014 Jan 27;17:63. doi: 10.11604/pamj.2014.17.63.3759. eCollection 2014.
9
Infantile osteopetrosis with superimposed rickets.婴儿型石骨症合并佝偻病。
Pediatr Radiol. 2013 Jan;43(2):189-95. doi: 10.1007/s00247-012-2511-2. Epub 2012 Nov 14.

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