Revia Steffie, Budzinska Magdalena A, Bogatyrova Olga, Neumann Felix, Zimmermann Astrid, Amendt Christiane, Albers Joachim
Research Unit Oncology, Merck Healthcare KGaA, Frankfurter Str. 250, 64293 Darmstadt, Germany.
Ardigen S.A., Podole 76, 30-394 Cracow, Poland.
Cancers (Basel). 2023 Dec 30;16(1):189. doi: 10.3390/cancers16010189.
Synovial sarcoma is a rare and highly aggressive subtype of soft tissue sarcoma. The clinical challenge posed by advanced or metastatic synovial sarcoma, marked by limited treatment options and suboptimal outcomes, necessitates innovative approaches. The topoisomerase II (Topo II) inhibitor doxorubicin has remained the cornerstone systemic treatment for decades, and there is pressing need for improved therapeutic strategies for these patients. This study highlights the potential to enhance the cytotoxic effects of doxorubicin within well-characterized synovial sarcoma cell lines using the potent and selective DNA-PK inhibitor, peposertib. In vitro investigations unveil a p53-mediated synergistic anti-tumor effect when combining doxorubicin with peposertib. The in vitro findings were substantiated by pronounced anti-tumor effects in mice bearing subcutaneously implanted tumors. A well-tolerated regimen for the combined application was established using both pegylated liposomal doxorubicin (PLD) and unmodified doxorubicin. Notably, the combination of PLD and peposertib displayed enhanced anti-tumor efficacy compared to unmodified doxorubicin at equivalent doses, suggesting an improved therapeutic window-a critical consideration for clinical translation. Efficacy studies in two patient-derived xenograft models of synovial sarcoma, accurately reflecting human metastatic disease, further validate the potential of this combined therapy. These findings align with previous evidence showcasing the synergy between DNA-PK inhibition and Topo II inhibitors in diverse tumor models, including breast and ovarian cancers. Our study extends the potential utility of combined therapy to synovial sarcoma.
滑膜肉瘤是软组织肉瘤中一种罕见且侵袭性很强的亚型。晚期或转移性滑膜肉瘤带来的临床挑战表现为治疗选择有限且预后欠佳,这就需要创新的治疗方法。几十年来,拓扑异构酶II(Topo II)抑制剂阿霉素一直是系统性治疗的基石,因此迫切需要为这些患者改进治疗策略。本研究强调了使用强效且选择性的DNA-PK抑制剂培唑帕尼增强阿霉素在特征明确的滑膜肉瘤细胞系中的细胞毒性作用的潜力。体外研究揭示了阿霉素与培唑帕尼联合使用时p53介导的协同抗肿瘤作用。在皮下植入肿瘤的小鼠中观察到的显著抗肿瘤作用证实了体外研究结果。使用聚乙二醇化脂质体阿霉素(PLD)和未修饰的阿霉素建立了一种耐受性良好的联合应用方案。值得注意的是,与同等剂量的未修饰阿霉素相比,PLD与培唑帕尼的联合应用显示出增强的抗肿瘤疗效,这表明治疗窗口有所改善——这是临床转化的一个关键考量因素。在两个准确反映人类转移性疾病的滑膜肉瘤患者来源的异种移植模型中的疗效研究进一步验证了这种联合疗法的潜力。这些发现与之前的证据一致,这些证据表明在包括乳腺癌和卵巢癌在内的多种肿瘤模型中,DNA-PK抑制与Topo II抑制剂之间存在协同作用。我们的研究将联合疗法的潜在应用扩展到了滑膜肉瘤。