Department of Dermatology, Center for Blistering Diseases, Tufts University School of Medicine, Boston, MA 02135.
Institut National de la Santé et de la Recherche Médicale, Centre de Recherche des Cordeliers, Sorbonne Université, Université de Paris, Paris F-75006, France.
Proc Natl Acad Sci U S A. 2024 Jan 30;121(5):e2317762121. doi: 10.1073/pnas.2317762121. Epub 2024 Jan 23.
Intravenous immunoglobulin (IVIg), a preparation of polyclonal serum IgG pooled from numerous blood donors, has been used for nearly three decades and is proving to be an efficient treatment for many autoimmune blistering diseases, including pemphigus vulgaris (PV). Despite its widespread use and therapeutic success, its mechanisms of action are not completely understood. Some of its anti-inflammatory and immunomodulatory actions have been studied. In this study, the authors present a twenty-year follow-up of 21 patients with clinical and immunopathological confirmed PV, treated with IVIg as monotherapy, according to an established published protocol. IVIg therapy produced long-term sustained, clinical, serological, and immunopathological remission. For 20 y, these patients received no drugs and experienced no disease. This observation suggests that there was the establishment of immune balance or restoration of immune regulation in these PV patients. Twelve (57%) patients experienced no relapse during follow-up. Six (29%) patients experienced a relapse due to acute stress or post-coronavirus infection and/or vaccination. Reinstitution of IVIg resulted in prompt sustained recovery. Three (14.2%) patients, in clinical and serological remission, died due to unrelated causes. No severe adverse effects from IVIg were documented in all 21 patients. The simultaneous or sequential anti-inflammatory and immunomodulatory effects of IVIg may have influenced the long-term clinical remission observed. This study provides a human prototype to examine the pathophysiology of autoimmunity and a model to study immune regulation and mechanisms that can facilitate restoring immune tolerance.
静脉注射免疫球蛋白(IVIg)是一种从众多献血者的混合血清中提取的多克隆 IgG 制剂,已使用近三十年,被证明是治疗多种自身免疫性水疱病的有效方法,包括寻常型天疱疮(PV)。尽管广泛使用且治疗效果显著,但它的作用机制尚未完全阐明。已经研究了其一些抗炎和免疫调节作用。在这项研究中,作者根据已发表的方案,对 21 例临床和免疫病理学确诊的 PV 患者进行了为期 20 年的随访,这些患者接受 IVIg 单药治疗。IVIg 治疗产生了长期持续的临床、血清学和免疫病理学缓解。20 年来,这些患者未接受任何药物治疗,也未出现疾病。这一观察结果表明,这些 PV 患者的免疫平衡得到了建立或免疫调节得到了恢复。12 例(57%)患者在随访期间无复发。6 例(29%)患者因急性应激或新冠病毒感染和/或接种疫苗而复发。重新给予 IVIg 导致迅速持续缓解。3 例(14.2%)处于临床和血清学缓解期的患者因非相关原因死亡。21 例患者均未发生 IVIg 严重不良反应。IVIg 的同时或序贯抗炎和免疫调节作用可能影响了观察到的长期临床缓解。这项研究为研究自身免疫的病理生理学提供了人类范例,并为研究免疫调节和恢复免疫耐受的机制提供了模型。