Pediatric Hematology, Oncology and Blood and Marrow Transplantation, Cleveland Clinic, Cleveland, Ohio; Blood and Marrow Transplant Program, Department of Hematology and Medical Oncology, Taussig Cancer Institute, Cleveland Clinic, Cleveland, Ohio.
Blood and Marrow Transplant Program, Department of Hematology and Medical Oncology, Taussig Cancer Institute, Cleveland Clinic, Cleveland, Ohio.
Transplant Cell Ther. 2024 May;30(5):534.e1-534.e13. doi: 10.1016/j.jtct.2024.02.002. Epub 2024 Feb 9.
The use of reduced-intensity conditioning (RIC) regimens has increased in an effort to minimize hematopoietic stem cell transplantation (HCT) end-organ toxicity, including gonadal toxicity. We aimed to describe the incidence of fertility potential and gonadal function impairment in adolescent and young adult survivors of HCT and to identify risk factors (including conditioning intensity) for impairment. We performed a multi-institutional, international retrospective cohort study of patients age 10 to 40 years who underwent first allogeneic HCT before December 1, 2019, and who were alive, in remission, and available for follow-up at 1 to 2 years post-HCT. For females, an AMH level of ≥.5 ng/mL defined preserved fertility potential; an AMH level of ≥.03 ng/mL was considered detectable. Gonadal failure was defined for females as an elevated follicle-stimulating hormone (FSH) level >30 mIU/mL with an estradiol (E2) level <17 pg/mL or current use of hormone replacement therapy (regardless of specific indication or intent). For males, gonadal failure was defined as an FSH level >10.4 mIU/mL or current use of hormone replacement therapy. A total of 326 patients (147 females) were available for analysis from 17 programs (13 pediatric, 4 adult). At 1 to 2 years post-HCT, 114 females (77.6%) had available FSH and E2 levels and 71 (48.3%) had available AMH levels. FSH levels were reported for 125 males (69.8%). Nearly all female HCT recipients had very low levels of AMH. One of 45 (2.2%) recipients of myeloablative conditioning (MAC) and four of 26 (15.4%) recipients of reduced-intensity conditioning (RIC) (P = .06) had an AMH ≥.5 ng/m, and 8 of 45 MAC recipients (17.8%) and 12 of 26 RIC recipients (46.2%) (P = .015) had a detectable AMH level. Total body irradiation (TBI) dose and cyclophosphamide equivalent dose (CED) were not associated with detectable AMH. The incidence of female gonadal hormone failure was 55.3%. In univariate analysis, older age at HCT was associated with greater likelihood of gonadal failure (median age, 17.6 versus 13.9; P < .0001), whereas conditioning intensity (RIC versus MAC), TBI, chronic graft-versus-host disease requiring systemic therapy, and CED were not significantly associated with gonadal function. In multivariable analysis, age remained statistically significant (odds ratio [OR]. 1.11; 95% confidence interval [CI], 1.03 to 1.22) for each year increase; P = .012), Forty-four percent of the males had gonadal failure. In univariate analysis, older age (median, 16.2 years versus 14.4 years; P = .0005) and TBI dose (P = .002) were both associated with gonadal failure, whereas conditioning intensity (RIC versus MAC; P = .06) and CED (P = .07) were not statistically significant. In multivariable analysis, age (OR, 1.16; 95% CI, 1.06-1.27 for each year increase; P = .0016) and TBI ≥600 cGy (OR, 6.23; 95% CI, 2.21 to 19.15; P = .0008) remained significantly associated with gonadal failure. Our data indicate that RIC does not significantly mitigate the risk for gonadal failure in females or males. Age at HCT and (specifically in males) TBI use seem to be independent predictors of post-transplantation gonadal function and fertility status. All patients should receive pre-HCT infertility counseling and be offered appropriate fertility preservation options and be screened post-HCT for gonadal failure.
使用强度降低的调理(RIC)方案的目的是尽量减少造血干细胞移植(HCT)的终末器官毒性,包括性腺毒性。我们旨在描述青少年和年轻成人 HCT 幸存者的生育潜力和性腺功能障碍的发生率,并确定损害的风险因素(包括调理强度)。我们对年龄在 10 至 40 岁之间、于 2019 年 12 月 1 日前接受首次异基因 HCT、存活、缓解且在 HCT 后 1 至 2 年可进行随访的患者进行了多机构、国际回顾性队列研究。对于女性,AMH 水平≥.5ng/ml 定义为保留生育潜力;AMH 水平≥.03ng/ml 被认为是可检测到的。对于女性,性腺功能衰竭定义为促卵泡激素(FSH)水平升高 >30mIU/ml,雌二醇(E2)水平 <17pg/ml,或目前正在使用激素替代疗法(无论具体指征或意图如何)。对于男性,性腺功能衰竭定义为 FSH 水平 >10.4mIU/ml 或目前正在使用激素替代疗法。共有来自 17 个项目(13 个儿科,4 个成人)的 326 名患者(147 名女性)可用于分析。在 HCT 后 1 至 2 年,114 名女性(77.6%)有可用的 FSH 和 E2 水平,71 名(48.3%)有可用的 AMH 水平。125 名男性(69.8%)报告了 FSH 水平。几乎所有接受 HCT 的女性患者的 AMH 水平都非常低。在 45 名接受骨髓清除性调理(MAC)的患者中,有 1 名(2.2%),在 26 名接受强度降低调理(RIC)的患者中,有 4 名(15.4%)(P=0.06)的 AMH≥.5ng/ml,在 45 名 MAC 接受者中有 8 名(17.8%)和 26 名 RIC 接受者中有 12 名(46.2%)(P=0.015)的 AMH 水平可检测到。全身照射(TBI)剂量和环磷酰胺等效剂量(CED)与可检测到的 AMH 无关。女性性腺激素衰竭的发生率为 55.3%。在单变量分析中,HCT 时年龄较大与性腺功能衰竭的可能性更大相关(中位数年龄,17.6 岁与 13.9 岁;P<0.0001),而调理强度(RIC 与 MAC)、TBI、需要系统治疗的慢性移植物抗宿主病和 CED 与性腺功能无关。在多变量分析中,年龄仍然具有统计学意义(比值比[OR],1.11;95%置信区间[CI],1.03 至 1.22),每增加一年;P=0.012),44%的男性存在性腺功能衰竭。在单变量分析中,年龄较大(中位数,16.2 岁与 14.4 岁;P=0.0005)和 TBI 剂量(P=0.002)与性腺功能衰竭均相关,而调理强度(RIC 与 MAC;P=0.06)和 CED(P=0.07)则无统计学意义。在多变量分析中,年龄(OR,1.16;95%CI,每增加一年增加 1.06-1.27;P=0.0016)和 TBI≥600cGy(OR,6.23;95%CI,2.21 至 19.15;P=0.0008)仍然与性腺功能衰竭显著相关。我们的数据表明,RIC 并不能显著降低女性或男性性腺功能衰竭的风险。HCT 时的年龄和(特别是在男性中)TBI 的使用似乎是移植后性腺功能和生育状况的独立预测因素。所有患者均应在 HCT 前接受不孕咨询,并提供适当的生育保护选择,并在 HCT 后进行性腺功能衰竭筛查。