Cincinnati Children's Hospital Medical Center, Cincinnati, OH, USA.
Department of Evolutionary Biology, University of Vienna, Vienna, Austria.
Nat Commun. 2024 Feb 12;15(1):1152. doi: 10.1038/s41467-024-45338-4.
The common human SNP rs3820282 is associated with multiple phenotypes including gestational length and likelihood of endometriosis and cancer, presenting a paradigmatic pleiotropic variant. Deleterious pleiotropic mutations cause the co-occurrence of disorders either within individuals, or across population. When adverse and advantageous effects are combined, pleiotropy can maintain high population frequencies of deleterious alleles. To reveal the causal molecular mechanisms of this pleiotropic SNP, we introduced this substitution into the mouse genome by CRISPR/Cas 9. Previous work showed that rs3820282 introduces a high-affinity estrogen receptor alpha-binding site at the Wnt4 locus. Here, we show that this mutation upregulates Wnt4 transcription in endometrial stroma, following the preovulatory estrogen peak. Effects on uterine transcription include downregulation of epithelial proliferation and induction of progesterone-regulated pro-implantation genes. We propose that these changes increase uterine permissiveness to embryo invasion, whereas they decrease resistance to invasion by cancer and endometriotic foci in other estrogen-responsive tissues.
常见的人类 SNP rs3820282 与多种表型相关,包括妊娠长度和子宫内膜异位症和癌症的可能性,呈现出典型的多效性变体。有害的多效性突变导致个体内部或人群中疾病的同时发生。当不利和有利的影响结合在一起时,多效性可以维持有害等位基因的高人口频率。为了揭示这种多效性 SNP 的因果分子机制,我们通过 CRISPR/Cas 9 将该取代物引入了小鼠基因组。先前的工作表明,rs3820282 在 Wnt4 基因座引入了一个高亲和力的雌激素受体 alpha 结合位点。在这里,我们表明该突变在上皮细胞增殖的下调和孕激素调节的着床前基因的诱导下,在子宫内膜基质中上调 Wnt4 转录。对子宫转录的影响包括上皮细胞增殖的下调和孕激素调节的着床前基因的诱导。我们提出,这些变化增加了子宫对胚胎侵袭的易感性,而减少了对其他雌激素反应性组织中癌症和子宫内膜异位症焦点侵袭的抵抗力。