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T大颗粒淋巴细胞白血病:一名发热、皮肤坏死性病变和血细胞减少的年轻女性的罕见诊断。

T-large Granular Lymphocytic Leukemia: A Rare Diagnosis in a Young Woman With Fever, Necrotic Skin Lesions and Cytopenias.

作者信息

Ferreira Mário, Paulo Joana, Ramos Paulo, Padrão Carolina, Neves Zélia

机构信息

Serviço de Medicina Interna, Hospital Professor Doutor Fernando Fonseca, Lisboa, PRT.

Serviço de Anatomia Patológica, Hospital Professor Doutor Fernando Fonseca, Lisboa, PRT.

出版信息

Cureus. 2024 Feb 2;16(2):e53468. doi: 10.7759/cureus.53468. eCollection 2024 Feb.

DOI:10.7759/cureus.53468
PMID:38435176
原文链接:https://pmc.ncbi.nlm.nih.gov/articles/PMC10909483/
Abstract

T-large granular lymphocytic leukemia (T-LGLL) is a rare lymphoproliferative disorder. The diagnosis is established by identifying an abnormally high number of clonal granular T lymphocytes in the peripheral blood and eventually in the bone marrow, in cases with medullary infiltration. The majority of patients present with symptoms related to neutropenia and this condition may be associated with autoimmune diseases in up to a third of cases. The authors describe the case of a 26-year-old patient admitted with subacute high fever and bullous dermatitis with necrotic lesions with central bullae. Analytically, she presented anemia and leukopenia with severe neutropenia of 200 cells/L. Skin lesions were compatible with ecthyma and the skin biopsy revealed aspects compatible with leukocytoclastic vasculitis. The myelogram and bone biopsy revealed hypoplasia of the myeloid line and a pathological T population of CD8+, TIA-1+ and granzyme B+, which were associated with compatible flow cytometry (CD3+, T-cell receptor (TCR) Alpha-Beta+, CD5+, CD2+, with loss of CD7 antigen expression) established the diagnosis of T-LGLL. The patient had a favorable evolution, with cytopenias almost returning to normal after two months. She began follow-up at a Hematology Reference Center, remaining asymptomatic without specific treatment considering the indolent course of the disease.

摘要

T 大颗粒淋巴细胞白血病(T-LGLL)是一种罕见的淋巴增殖性疾病。诊断通过在外周血中识别出异常大量的克隆性颗粒 T 淋巴细胞来确立,在骨髓浸润的病例中最终要在骨髓中识别。大多数患者表现出与中性粒细胞减少相关的症状,在多达三分之一的病例中,这种情况可能与自身免疫性疾病有关。作者描述了一名 26 岁患者的病例,该患者因亚急性高热和伴有中央大疱的坏死性病变的大疱性皮炎入院。分析显示,她出现贫血和白细胞减少,严重中性粒细胞减少至 200 个细胞/升。皮肤病变与深脓疱病相符,皮肤活检显示与白细胞破碎性血管炎相符的表现。骨髓检查和骨髓活检显示髓系发育不全以及 CD8 +、TIA-1 + 和颗粒酶 B + 的病理性 T 细胞群,这与相符的流式细胞术结果(CD3 +、T 细胞受体(TCR)α-β +、CD5 +、CD2 +,伴有 CD7 抗原表达缺失)共同确立了 T-LGLL 的诊断。患者病情进展良好,两个月后血细胞减少几乎恢复正常。她开始在血液学参考中心进行随访,考虑到疾病进展缓慢,在未进行特殊治疗的情况下一直无症状。

https://cdn.ncbi.nlm.nih.gov/pmc/blobs/2362/10909483/474c467db802/cureus-0016-00000053468-i07.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/2362/10909483/41a6dc140dd1/cureus-0016-00000053468-i01.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/2362/10909483/02fdca431869/cureus-0016-00000053468-i02.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/2362/10909483/b4e3365bccc5/cureus-0016-00000053468-i03.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/2362/10909483/77bea416e289/cureus-0016-00000053468-i04.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/2362/10909483/7c8c25f0de87/cureus-0016-00000053468-i05.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/2362/10909483/34802ff07b05/cureus-0016-00000053468-i06.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/2362/10909483/474c467db802/cureus-0016-00000053468-i07.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/2362/10909483/41a6dc140dd1/cureus-0016-00000053468-i01.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/2362/10909483/02fdca431869/cureus-0016-00000053468-i02.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/2362/10909483/b4e3365bccc5/cureus-0016-00000053468-i03.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/2362/10909483/77bea416e289/cureus-0016-00000053468-i04.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/2362/10909483/7c8c25f0de87/cureus-0016-00000053468-i05.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/2362/10909483/34802ff07b05/cureus-0016-00000053468-i06.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/2362/10909483/474c467db802/cureus-0016-00000053468-i07.jpg

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本文引用的文献

1
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Hemasphere. 2021 Jun 1;5(6):e573. doi: 10.1097/HS9.0000000000000573. eCollection 2021 Jun.
2
T cell large granular lymphocyte leukemia and chronic NK lymphocytosis.T 细胞大颗粒淋巴细胞白血病与慢性 NK 淋巴细胞增生症。
Best Pract Res Clin Haematol. 2019 Sep;32(3):207-216. doi: 10.1016/j.beha.2019.06.006. Epub 2019 Jun 22.
3
Latest Advances in the Diagnosis and Treatment of Large Granular Lymphocytic Leukemia.
大颗粒淋巴细胞白血病诊断与治疗的最新进展
Am Soc Clin Oncol Educ Book. 2018 May 23;38:616-625. doi: 10.1200/EDBK_200689.
4
Large granular lymphocytic leukemia. Current diagnostic and therapeutic approaches and novel treatment options.大颗粒淋巴细胞白血病。当前的诊断和治疗方法及新的治疗选择。
Expert Rev Hematol. 2017 Mar;10(3):251-258. doi: 10.1080/17474086.2017.1284585. Epub 2017 Jan 29.
5
Somatic STAT3 mutations in large granular lymphocytic leukemia.大颗粒淋巴细胞白血病中的体细胞 STAT3 突变。
N Engl J Med. 2012 May 17;366(20):1905-13. doi: 10.1056/NEJMoa1114885.
6
Analysis of a French cohort of patients with large granular lymphocyte leukemia: a report on 229 cases.分析法国大颗粒淋巴细胞白血病患者队列:229 例报告。
Haematologica. 2010 Sep;95(9):1534-41. doi: 10.3324/haematol.2009.018481. Epub 2010 Apr 7.
7
Characteristic appearances of the bone marrow in T-cell large granular lymphocyte leukaemia.T细胞大颗粒淋巴细胞白血病的骨髓特征性表现。
Histopathology. 2007 Apr;50(5):547-54. doi: 10.1111/j.1365-2559.2007.02656.x.
8
Large granular lymphocyte leukemia.大颗粒淋巴细胞白血病
Oncologist. 2006 Mar;11(3):263-73. doi: 10.1634/theoncologist.11-3-263.
9
Clinical features of large granular lymphocyte leukemia.大颗粒淋巴细胞白血病的临床特征。
Semin Hematol. 2003 Jul;40(3):185-95. doi: 10.1016/s0037-1963(03)00133-1.
10
Clonal diseases of large granular lymphocytes.大颗粒淋巴细胞的克隆性疾病。
Blood. 1993 Jul 1;82(1):1-14.