Haque Arinil, Annas Jimmy Yanuar
Residence, Department of Obstetric and gynecologic, Faculty of Medicine, Airlangga University, Dr. Soetomo Hospital Surabaya, Indonesia.
Fertility Divison Staff, Obstetric and gynecologic Airlangga, Indonesia.
Int J Surg Case Rep. 2024 Apr;117:109435. doi: 10.1016/j.ijscr.2024.109435. Epub 2024 Feb 28.
This study aimed to characterize unicornuate uterus with noncommunicating horns, an uncommon Müllerian abnormality. With a 0.06 % incidence rate, this disorder can lead to endometriosis linked to retrograde menstruation or hematometra, which can cause significant pelvic pain.
A 39-year-old woman with chief complaints of severe dysmenorrhea for five years. Despite receiving hormone therapy, the patient's symptoms persisted. She has only one living child born at laparotomy for an abdominal pregnancy 19 years ago. Upon ultrasound inspection, a 2.8 × 3 cm endometrioma was the only finding. Prior to her laparoscopic procedure, the woman had a unicornuate uterus on her right side with a normal cervix, and also a non-communicating hemiuterus in her left horn that had burst due to adhesion separation and was leaking chocolate fluid. On the left side, there was also a 3 × 3 cm endometrioma. Following that, a laparoscopic hysterectomy was carried out.
Although misread occasionally, the correct diagnosis of a unicornuate uterus with a noncommunicating horn is clinically important. The history of this patient's abdominal pregnancy may have developed in the rudimentary horn after sperm or fertilized eggs moved trans peritoneally, with life-threatening consequences if ruptured. This patient developed severe dysmenorrhea after receiving hormonal therapy, possibly caused by a noncommunicating left horn uterine hematometra and endometrioma. In this case, a laparoscopic hysterectomy was afterward chosen due to the patient's request according to her symptoms.
Unicornuate uterine with non-communicating horns is scarce however may cause severe complications. Considered a treatment to prevent related morbidity, laparoscopy is necessary to affirm the diagnosis.
本研究旨在对单角子宫合并非交通性残角这一罕见的苗勒管异常进行特征描述。该疾病发病率为0.06%,可导致与逆行月经或子宫积血相关的子宫内膜异位症,进而引起严重的盆腔疼痛。
一名39岁女性,主要症状为严重痛经五年。尽管接受了激素治疗,患者症状仍持续存在。她仅有一个存活子女,19年前因腹腔妊娠行剖腹手术分娩。超声检查仅发现一个2.8×3厘米的子宫内膜瘤。在腹腔镜手术前,该女性右侧为单角子宫,宫颈正常,左侧残角子宫因粘连分离破裂,有巧克力样液体渗漏。左侧还有一个3×3厘米的子宫内膜瘤。随后,实施了腹腔镜子宫切除术。
尽管偶尔会出现误诊,但正确诊断单角子宫合并非交通性残角在临床上具有重要意义。该患者腹腔妊娠史可能是精子或受精卵经腹腔移动至残角后发生的,如果破裂会危及生命。该患者接受激素治疗后出现严重痛经,可能是由左侧非交通性残角子宫积血和子宫内膜瘤所致。在此病例中,根据患者症状及要求,随后选择了腹腔镜子宫切除术。
单角子宫合并非交通性残角较为罕见,但可能导致严重并发症。腹腔镜检查对于确诊及预防相关发病至关重要,是一种必要的治疗手段。