Atypical refractory occipital neuralgia treated with a unilateral dual-lead occipital nerve stimulator: a case report.

To describe the successful treatment of atypical occipital neuralgia (ON) using a unilateral dual-lead occipital nerve stimulator. Outpatient clinic/operating room. A 53-year-old male with atypical ON. Patient was previously diagnosed with treatment-refractory left-sided trigeminal neuralgia with atypical occipital distribution. On presentation, his symptoms were consistent with ON with distribution to the left fronto-orbital area. He received a left-sided nerve stimulator implant targeting both the greater and lesser occipital nerves. Patient reported pain relief from a numerical rating scale 10/10 to 3-4/10. ON with referred ipsilateral trigeminal distribution should be considered when patients present with simultaneous facial and occipital pain. Further, a dual-lead unilateral stimulator approach may be a viable treatment.