Xi'an Institute of Hematology, Xi'an Central Hospital Affiliated to Xi'an Jiaotong University, Xi'an, Shaanxi, China.
Department of Hematology, Tianjin Hospital, Tianjin, China.
J Int Med Res. 2024 Jul;52(7):3000605241266221. doi: 10.1177/03000605241266221.
Raising awareness of acquired hemophilia A (AHA) and early diagnosis is critical to reduce the associated mortality rate. We aimed to characterize acquired hemophilia in Chinese patients and evaluate the effectiveness of immunotherapy.
The clinical characteristics, laboratory test data, therapeutic approaches, and outcomes of 20 patients with AHA who were admitted to Xi'an Central Hospital between January 2012 and December 2020 were retrospectively studied.
Nine of the patients (45%) were treated by single glucocorticoid administration; three (15%) with cyclophosphamide (CP) in combination with a glucocorticoid; four individuals (20%) received a combination therapy of rituximab with CP and glucocorticoid or rituximab with CP, vincristine, and a glucocorticoid; three (15%) by injection of human immunoglobulin in combination with a glucocorticoid; and one (5%) with CP alone. Six patients (30%) achieved total remission and 11 (55%) partial remission (PR), but three (15%) did not enter remission, indicating an objective response rate of 85%.
Combination therapy with rituximab or intravenous human immunoglobulin achieves superior results in some patients with AHA. Immunosuppression and the administration of coagulation factors can rapidly control the disease and are efficacious, but >50% of patients only achieved PR. These findings suggest that the complete elimination of inhibitors requires prolonged immunosuppression therapy.
提高对获得性血友病 A(AHA)的认识并早期诊断对于降低相关死亡率至关重要。我们旨在描述中国患者获得性血友病的特征,并评估免疫疗法的效果。
回顾性研究了 2012 年 1 月至 2020 年 12 月期间在西安中心医院就诊的 20 例 AHA 患者的临床特征、实验室检查数据、治疗方法和结局。
9 例患者(45%)接受单一糖皮质激素治疗;3 例(15%)接受环磷酰胺(CP)联合糖皮质激素治疗;4 例(20%)接受利妥昔单抗联合 CP 和糖皮质激素或利妥昔单抗联合 CP、长春新碱和糖皮质激素治疗;3 例(15%)接受糖皮质激素联合人免疫球蛋白注射治疗;1 例(5%)接受 CP 单药治疗。6 例患者(30%)达到完全缓解,11 例(55%)部分缓解(PR),但 3 例(15%)未缓解,客观缓解率为 85%。
利妥昔单抗或静脉用人免疫球蛋白联合治疗在某些 AHA 患者中效果较好。免疫抑制和凝血因子的给予可以迅速控制疾病且有效,但>50%的患者仅获得 PR。这些发现表明,要完全消除抑制剂需要进行长期的免疫抑制治疗。