• 文献检索
  • 文档翻译
  • 深度研究
  • 学术资讯
  • Suppr Zotero 插件Zotero 插件
  • 邀请有礼
  • 套餐&价格
  • 历史记录
应用&插件
Suppr Zotero 插件Zotero 插件浏览器插件Mac 客户端Windows 客户端微信小程序
定价
高级版会员购买积分包购买API积分包
服务
文献检索文档翻译深度研究API 文档MCP 服务
关于我们
关于 Suppr公司介绍联系我们用户协议隐私条款
关注我们

Suppr 超能文献

核心技术专利:CN118964589B侵权必究
粤ICP备2023148730 号-1Suppr @ 2026

文献检索

告别复杂PubMed语法,用中文像聊天一样搜索,搜遍4000万医学文献。AI智能推荐,让科研检索更轻松。

立即免费搜索

文件翻译

保留排版,准确专业,支持PDF/Word/PPT等文件格式,支持 12+语言互译。

免费翻译文档

深度研究

AI帮你快速写综述,25分钟生成高质量综述,智能提取关键信息,辅助科研写作。

立即免费体验

成人发作的周期性发热、咽炎、颌下腺炎和皮疹综合征:秋水仙碱治疗成功。

Adult-Onset PFAPA Syndrome: Successful Management with Colchicine.

机构信息

Division of Rheumatology, Saint Louis University School of Medicine, Saint Louis, MO, USA.

Department of Medicine, Quaid e Azam Medical College, Bahawalpur, Pakistan.

出版信息

Am J Case Rep. 2024 Aug 29;25:e943658. doi: 10.12659/AJCR.943658.

DOI:10.12659/AJCR.943658
PMID:39205369
原文链接:https://pmc.ncbi.nlm.nih.gov/articles/PMC11370285/
Abstract

BACKGROUND Periodic fever, aphthous stomatitis, pharyngitis, and cervical adenitis (PFAPA) syndrome is an autoinflammatory fever syndrome primarily seen in children under age 5 years, and its etiology is unknown. Most cases are resolved by the age of 10 years, and it is rare in adults. PFAPA is characterized by recurrent episodes of fever associated with pharyngitis, stomatitis, and cervical adenitis, although not all clinical features are present at initial evaluation. Diagnosis is made clinically, as there are no specific biomarkers available. Treatment includes prednisone, colchicine, interleukin-1 blockers, and tonsillectomy. We report a case of adult-onset PFAPA syndrome that responded to colchicine. CASE REPORT A 22-year-old woman presented to the Rheumatology Clinic for evaluation of recurrent fevers associated with sore throat and enlarged painful cervical lymph nodes. She was symptom-free between the episodes. Workup for infectious causes and autoinflammatory/autoimmune diseases was unremarkable. Various differential diagnoses were considered, due to her unusual presentation. After all were ruled out, PFAPA was diagnosed based on her symptoms, and she started steroids, to which she had a dramatic response and resolution of symptoms. She was then transitioned to oral colchicine, which significantly decreased flare frequency. CONCLUSIONS Being aware of PFAPA syndrome in adults is vital. A timely diagnosis can significantly improve a patient's quality of life. This case highlights the importance of considering PFAPA syndrome in the differential diagnosis of periodic febrile illnesses in adults and the role of Colchicine as prophylaxis. Larger studies are needed to understand etiopathogenesis better and develop other effective therapeutics.

摘要

背景

周期性发热、口疮性口炎、咽炎和颈部淋巴结炎(PFAPA)综合征是一种主要发生在 5 岁以下儿童的自身炎症性发热综合征,其病因不明。大多数病例在 10 岁时得到解决,在成年人中很少见。PFAPA 的特征是反复出现发热,伴有咽炎、口疮性口炎和颈部淋巴结炎,尽管初始评估时并非所有临床特征都存在。由于没有特异性生物标志物,因此通过临床诊断。治疗包括泼尼松、秋水仙碱、白细胞介素-1 阻滞剂和扁桃体切除术。我们报告一例成人发病的 PFAPA 综合征,对秋水仙碱有反应。

病例报告

一名 22 岁女性因反复发热伴有咽痛和增大的疼痛性颈部淋巴结就诊于风湿病诊所。她在发作之间无症状。感染原因和自身炎症/自身免疫性疾病的检查均无异常。由于她的不寻常表现,考虑了各种不同的诊断。在排除所有其他诊断后,根据她的症状诊断为 PFAPA,她开始接受类固醇治疗,症状明显缓解。然后她转为口服秋水仙碱,显著降低了发作频率。

结论

了解成人中的 PFAPA 综合征至关重要。及时诊断可以显著提高患者的生活质量。本病例强调了在成人周期性发热疾病的鉴别诊断中考虑 PFAPA 综合征的重要性,以及秋水仙碱作为预防药物的作用。需要更大的研究来更好地了解病因发病机制并开发其他有效的治疗方法。

相似文献

1
Adult-Onset PFAPA Syndrome: Successful Management with Colchicine.成人发作的周期性发热、咽炎、颌下腺炎和皮疹综合征:秋水仙碱治疗成功。
Am J Case Rep. 2024 Aug 29;25:e943658. doi: 10.12659/AJCR.943658.
2
Is colchicine an effective treatment in periodic fever, aphtous stomatitis, pharyngitis, cervical adenitis (PFAPA) syndrome?秋水仙碱对周期性发热、阿弗他口炎、咽炎、颈淋巴结炎(PFAPA)综合征有效吗?
Joint Bone Spine. 2016 Jul;83(4):406-11. doi: 10.1016/j.jbspin.2015.08.017. Epub 2016 Apr 7.
3
Adult-onset Periodic Fever, Aphthous Stomatitis, Pharyngitis and Cervical Adenitis Syndrome Responsive to Colchicine.对秋水仙碱有反应的成人发作性发热、口疮性口炎、咽炎和颈淋巴结炎综合征。
Intern Med. 2023 Dec 1;62(23):3555-3558. doi: 10.2169/internalmedicine.1364-22. Epub 2023 Apr 14.
4
Disease phenotypes in adult patients with suspected undifferentiated autoinflammatory diseases and PFAPA syndrome: Clinical and therapeutic implications.疑似未分化自身炎症性疾病和 PFAPA 综合征的成年患者的疾病表型:临床和治疗意义。
Autoimmun Rev. 2024 Jul-Aug;23(7-8):103520. doi: 10.1016/j.autrev.2024.103520. Epub 2024 Mar 30.
5
Gray zone in the spectrum of autoinflammatory diseases: familial Mediterranean fever accompanying periodic fever, aphthous stomatitis, pharyngitis, and adenitis syndrome: single-center experience.自身炎症性疾病谱中的灰色地带:家族性地中海热伴周期性发热、口腔溃疡、咽炎和淋巴结炎综合征:单中心经验。
Eur J Pediatr. 2023 Dec;182(12):5473-5482. doi: 10.1007/s00431-023-05209-4. Epub 2023 Sep 30.
6
Pregnancy complicated with PFAPA (periodic fever, aphthous stomatitis, pharyngitis and cervical adenitis) syndrome: a case report.妊娠合并 PFAPA(周期性发热、口疮性口炎、咽炎和颈淋巴结炎)综合征:病例报告。
BMC Pregnancy Childbirth. 2018 Jun 4;18(1):207. doi: 10.1186/s12884-018-1854-6.
7
[PFAPA syndrome - An important differential diagnosis in children with recurrent fever].[PFAPA综合征——儿童反复发热的重要鉴别诊断]
Lakartidningen. 2019 Oct 29;116:FP9U.
8
Clinical features and new diagnostic criteria for the syndrome of periodic fever, aphthous stomatitis, pharyngitis, and cervical adenitis.周期性发热、口疮性口炎、咽炎和颈淋巴结炎综合征的临床特征和新的诊断标准。
Int J Rheum Dis. 2019 Aug;22(8):1489-1497. doi: 10.1111/1756-185X.13610. Epub 2019 May 27.
9
Challenges in the diagnosis of periodic fever, aphthous stomatitis, pharyngitis, and adenitis syndrome in developing countries-A decade of experience from North India.发展中国家周期性发热、口疮性口炎、咽炎和淋巴结炎综合征诊断中的挑战——来自印度北部的十年经验。
Front Immunol. 2022 Sep 20;13:958473. doi: 10.3389/fimmu.2022.958473. eCollection 2022.
10
Exploring factors for predicting colchicine responsiveness in children with PFAPA.探讨预测儿童 PFAPA 对秋水仙碱反应的因素。
Eur J Pediatr. 2024 Oct;183(10):4337-4343. doi: 10.1007/s00431-024-05703-3. Epub 2024 Jul 31.

本文引用的文献

1
Disease phenotypes in adult patients with suspected undifferentiated autoinflammatory diseases and PFAPA syndrome: Clinical and therapeutic implications.疑似未分化自身炎症性疾病和 PFAPA 综合征的成年患者的疾病表型:临床和治疗意义。
Autoimmun Rev. 2024 Jul-Aug;23(7-8):103520. doi: 10.1016/j.autrev.2024.103520. Epub 2024 Mar 30.
2
Adult-onset Periodic Fever, Aphthous Stomatitis, Pharyngitis and Cervical Adenitis Syndrome Responsive to Colchicine.对秋水仙碱有反应的成人发作性发热、口疮性口炎、咽炎和颈淋巴结炎综合征。
Intern Med. 2023 Dec 1;62(23):3555-3558. doi: 10.2169/internalmedicine.1364-22. Epub 2023 Apr 14.
3
Periodic fever, aphthous stomatitis, pharyngitis, and adenitis (PFAPA) syndrome: A review.周期性发热、阿弗他口炎、咽炎和腺炎(PFAPA)综合征:综述
World J Otorhinolaryngol Head Neck Surg. 2021 Jun 27;7(3):166-173. doi: 10.1016/j.wjorl.2021.05.004. eCollection 2021 Jul.
4
Periodic Fever, Aphthous Stomatitis, Pharyngitis, and Cervical Adenitis Syndrome: A Rare Etiology of Fever in Adults.周期性发热、阿弗他口炎、咽炎和颈淋巴结炎综合征:成人发热的罕见病因
Cureus. 2021 Apr 29;13(4):e14749. doi: 10.7759/cureus.14749.
5
Children and Adults with PFAPA Syndrome: Similarities and Divergences in a Real-Life Clinical Setting.儿童和成人 PFAPA 综合征:真实临床环境中的相似与差异。
Adv Ther. 2021 Feb;38(2):1078-1093. doi: 10.1007/s12325-020-01576-8. Epub 2020 Dec 14.
6
The Role of Matrix Metalloproteinases in Periodontal Disease.基质金属蛋白酶在牙周病中的作用。
Int J Environ Res Public Health. 2020 Jul 8;17(14):4923. doi: 10.3390/ijerph17144923.
7
A Case of Adult-Onset Periodic Fever, Aphthous Stomatitis, Pharyngitis, and Cervical Adenitis (PFAPA) Syndrome Responsive to Tonsillectomy in Japan.日本一例成人起病的周期性发热、阿弗他口炎、咽炎和颈淋巴结炎(PFAPA)综合征对扁桃体切除术有反应
Case Rep Otolaryngol. 2019 Sep 16;2019:1746180. doi: 10.1155/2019/1746180. eCollection 2019.
8
Periodic fever, aphthous stomatitis, pharyngitis, and cervical adenitis (PFAPA) syndrome: main features and an algorithm for clinical practice.周期性发热、口疮性口炎、咽炎和颈淋巴结炎(PFAPA)综合征:主要特征和临床实践算法。
Rheumatol Int. 2019 Jun;39(6):957-970. doi: 10.1007/s00296-019-04257-0. Epub 2019 Feb 23.
9
Treatment options for periodic fever, aphthous stomatitis, pharyngitis, and cervical adenitis (PFAPA) syndrome in children and adults: a narrative review.儿童和成人复发性发热、口腔溃疡、咽炎和颈淋巴结炎(PFAPA)综合征的治疗选择:叙述性综述。
Clin Rheumatol. 2019 Jan;38(1):11-17. doi: 10.1007/s10067-018-4361-2. Epub 2018 Nov 28.
10
Pregnancy complicated with PFAPA (periodic fever, aphthous stomatitis, pharyngitis and cervical adenitis) syndrome: a case report.妊娠合并 PFAPA(周期性发热、口疮性口炎、咽炎和颈淋巴结炎)综合征:病例报告。
BMC Pregnancy Childbirth. 2018 Jun 4;18(1):207. doi: 10.1186/s12884-018-1854-6.