Nakazawa Yasutaka, Ishida Mitsuaki, Sekine Kazuomi, Shimada Fumio, Suzuki Tomio, Hirose Yoshinobu
Department of Pathology, Osaka Medical and Pharmaceutical University, Takatsuki, Osaka 569-8686, Japan.
Department of General Medicine, Osaka Medical and Pharmaceutical University, Takatsuki, Osaka 569-8686, Japan.
Biomed Rep. 2024 Aug 19;21(5):148. doi: 10.3892/br.2024.1836. eCollection 2024 Nov.
Mesenteric panniculitis (MP), also known as sclerosing mesenteritis, is a rare idiopathic condition characterised by chronic inflammation and fibrosis in the mesentery. While small amounts of chylous ascites due to lymph drainage obstruction are not rare in patients with MP, massive ascites is a rare complication. Moreover, protein-losing enteropathy (PLE), a rare intestinal condition of uncompensated plasma protein loss, can occur in patients with MP. To the best of our knowledge, the present study is the first to report MP with massive chylous pleural effusion and PLE in a 56-year-old male presenting with dyspnoea at Osaka Medical and Pharmaceutical University Hospital (Osaka, Japan) in March 2023. Approximately 5 years prior, the patient noticed systemic oedema, transient abdominal pain and fever and weight loss, and was diagnosed with chylous ascites and PLE by abdominal paracentesis and endoscopic examination of the small intestine. Although initial prednisolone (20 mg/day) administration improved the oedema gradual and uncontrolled fluid buildup was observed. Computed tomography revealed pneumothorax, bilateral massive pleural effusion, and pneumonia. Despite extensive antibiotic therapy [voriconazole (300 mg, twice/day), Ampicillin/Sulbactam (3 g x 4/day), and Vancomycin (1,000 mg x 2/day)], the patient succumbed to respiratory failure 1 month later. Autopsy revealed massive chylous ascites, pleural effusion and the presence of thickened and calcified nodules in the mesentery. Histopathological examination showed diffuse fat necrosis with fibrosclerosis, calcification and lymphocytic infiltration within the mesentery. Therefore, a definitive diagnosis of MP was made. The present case highlighted the importance of considering MP as a differential diagnosis in cases of concurrent chylous ascites, pleural effusion and PLE in patients with abdominal pain, fever and weight loss.
肠系膜脂膜炎(MP),也称为硬化性肠系膜炎症,是一种罕见的特发性疾病,其特征为肠系膜的慢性炎症和纤维化。虽然MP患者因淋巴引流受阻出现少量乳糜性腹水并不少见,但大量腹水是一种罕见的并发症。此外,蛋白丢失性肠病(PLE),一种罕见的未代偿性血浆蛋白丢失的肠道疾病,也可能发生在MP患者中。据我们所知,本研究首次报道了2023年3月在日本大阪医科药科大学医院(大阪)一名56岁男性因呼吸困难就诊时出现大量乳糜性胸腔积液和PLE的MP病例。大约5年前,患者出现全身性水肿、短暂性腹痛、发热和体重减轻,通过腹腔穿刺和小肠内镜检查诊断为乳糜性腹水和PLE。尽管最初给予泼尼松龙(20毫克/天)治疗后水肿有所改善,但仍观察到液体逐渐积聚且无法控制。计算机断层扫描显示气胸、双侧大量胸腔积液和肺炎。尽管进行了广泛的抗生素治疗[伏立康唑(300毫克,每日两次)、氨苄西林/舒巴坦(3克×4/天)和万古霉素(1000毫克×2/天)],患者1个月后死于呼吸衰竭。尸检显示大量乳糜性腹水、胸腔积液以及肠系膜中存在增厚和钙化的结节。组织病理学检查显示肠系膜内弥漫性脂肪坏死伴纤维硬化、钙化和淋巴细胞浸润。因此,确诊为MP。本病例强调了在腹痛、发热和体重减轻的患者同时出现乳糜性腹水、胸腔积液和PLE时,将MP作为鉴别诊断的重要性。