Hyodo Toshiki, Hara Shigeo, Goto Shunsuke, Fujii Hideki, Nishi Shinichi, Yoshimoto Akihiro, Itoh Tomoo
Department of Diagnostic Pathology, Kobe University Graduate School of Medicine, Kobe, Japan.
Department of Diagnostic Pathology, Kobe City Medical Center General Hospital, Kobe, Japan.
Virchows Arch. 2025 May;486(5):991-1000. doi: 10.1007/s00428-024-03921-6. Epub 2024 Sep 9.
Neural epidermal growth factor-like 1 protein (NELL1) is the second most common target antigen in membranous glomerulonephritis (MGN). However, data regarding the clinicopathological characteristics of NELL1-associated MGN are limited owing to its low prevalence. This study examined the prevalence and clinicopathological characteristics of NELL1-associated MGN in a Japanese cohort. Additionally, we compared the clinicopathological features of NELL1-positive MGN, phospholipase A2 receptor 1 (PLA2R1)-positive MGN, and MGN negative for all three antigens (NELL1, PLA2R1, and thrombospondin type-1 domain-containing 7A). Among 257 consecutive patients pathologically diagnosed with MGN at two centers in Japan, 24 (9.3%) were immunohistochemically positive for NELL1. Clinically, patients with NELL1-positive MGN were significantly older (p < 0.001) and had a higher frequency of bucillamine use (vs PLA2R1-positive MGN, p < 0.01). Histologically, NELL1-positive MGN exhibited significantly lower detection of spikes and crater formation (p < 0.001), higher prevalence of segmental spike distribution (vs PLA2R1-positive MGN: p < 0.001), and higher prevalence of stage I cases on electron microscopy (p < 0.01). There were no significant differences in the prognoses among the three groups. The characteristic histological feature of segmental distribution in NELL1-positive MGN may be related to bucillamine use and the early phase of the disease. Further investigations with larger numbers of patients may offer further insight into the prognosis of patients with NELL1-positive MGN.
神经表皮生长因子样1蛋白(NELL1)是膜性肾小球肾炎(MGN)中第二常见的靶抗原。然而,由于其患病率较低,关于NELL1相关MGN临床病理特征的数据有限。本研究调查了日本队列中NELL1相关MGN的患病率和临床病理特征。此外,我们比较了NELL1阳性MGN、磷脂酶A2受体1(PLA2R1)阳性MGN以及三种抗原(NELL1、PLA2R1和含血小板反应蛋白1型结构域7A)均为阴性的MGN的临床病理特征。在日本两个中心连续257例经病理诊断为MGN的患者中,24例(9.3%)免疫组化检测NELL1呈阳性。临床上,NELL1阳性MGN患者年龄显著更大(p<0.001),使用布西拉明的频率更高(与PLA2R1阳性MGN相比,p<0.01)。组织学上,NELL1阳性MGN的钉突和火山口形成检出率显著更低(p<0.001),节段性钉突分布患病率更高(与PLA2R1阳性MGN相比:p<0.001),电镜下I期病例患病率更高(p<0.01)。三组之间的预后无显著差异。NELL1阳性MGN节段性分布的特征性组织学特征可能与布西拉明的使用和疾病早期阶段有关。对更多患者进行进一步研究可能会为NELL1阳性MGN患者的预后提供更多见解。