Lee Hong Lyeol, Kim Lucia, Lee Kyung Hee, Kim Cheol-Woo
Department of Internal Medicine, Inha University College of Medicine, Incheon, South Korea.
Department of Pathology, Inha University College of Medicine, Incheon, South Korea.
Respir Med Case Rep. 2024 Aug 22;51:102095. doi: 10.1016/j.rmcr.2024.102095. eCollection 2024.
Nodules and cysts with upper lobe predominance on chest computed tomography (CT) are highly suggestive of pulmonary Langerhans cell histiocytosis (PLCH). Herein, we describe a case of PLCH that presented with the unusual CT findings of subpleural ground-glass opacity (GGO) and traction bronchiectasis mostly in both lower lungs. No nodules or cysts were observed in the upper or middle lung areas. Video-assisted thoracoscopic biopsies were performed at the right lower lobe. Biopsy specimens showed findings consistent with those of scarred PLCH. To the best of our knowledge, this is the first case of PLCH presenting as GGO in the lower lungs.
胸部计算机断层扫描（CT）显示上叶为主的结节和囊肿高度提示肺朗格汉斯细胞组织细胞增多症（PLCH）。在此，我们描述一例PLCH病例，其胸部CT表现不寻常，主要为两下肺胸膜下磨玻璃影（GGO）和牵拉性支气管扩张。上肺和中肺区域未观察到结节或囊肿。在右下叶进行了电视辅助胸腔镜活检。活检标本显示的结果与瘢痕性PLCH一致。据我们所知，这是首例表现为下肺GGO的PLCH病例。
