Moro Naoki, Nakajima Masanori, Shozawa Hidenobu, Nagai Kentaro, Uchibori Ayumi, Ichikawa Yaeko
Department of Neurology, Kyorin University Hospital.
Rinsho Shinkeigaku. 2024 Oct 29;64(10):714-718. doi: 10.5692/clinicalneurol.cn-001977. Epub 2024 Oct 26.
We studied the clinical features of five Japanese cases with leucine-rich glioma inactivated-1 (LGI1) antibody-positive encephalitis. Their symptoms included seizures, hallucinations, memory impairment, apathy, anxiety, agitation, faciobrachial dystonic seizure (FBDS), and ictal piloerection. All five patients showed hippocampal fluid attenuated inversion recovery (FLAIR) hyperintensity on brain MRI even though their cell counts of cerebrospinal fluid (CSF) were normal range. Four patients had syndrome of inappropriate secretion of antidiuretic hormone. One patient with FBDS also showed basal ganglia lesion on her brain MRI. Sodium channel blockers apparently lowered the frequency of FBDS. One patient had a thyroid cancer and underwent thyroidectomy. Substantial response to immunotherapy was seen in four out of five cases. At follow-up ≥2 years, all five patients had never relapsed. In cases of limbic encephalitis with normal CSF cell counts and hyponatremia, we should consider LGI1 antibody-positive encephalitis and conduct immunotherapy immediately.
我们研究了5例富含亮氨酸胶质瘤失活1(LGI1)抗体阳性脑炎的日本患者的临床特征。他们的症状包括癫痫发作、幻觉、记忆障碍、冷漠、焦虑、躁动、面臂肌张力障碍性发作(FBDS)和发作期竖毛。尽管所有5例患者的脑脊液细胞计数在正常范围内,但脑部MRI均显示海马液体衰减反转恢复(FLAIR)高信号。4例患者出现抗利尿激素分泌不当综合征。1例FBDS患者脑部MRI还显示基底节病变。钠通道阻滞剂明显降低了FBDS的发作频率。1例患者患有甲状腺癌并接受了甲状腺切除术。5例中有4例对免疫治疗有显著反应。在≥2年的随访中,所有5例患者均未复发。对于脑脊液细胞计数正常且低钠血症的边缘性脑炎病例,我们应考虑LGI1抗体阳性脑炎并立即进行免疫治疗。