Tetsuka Syuichi, Suzuki Tomohiro, Ogawa Tomoko, Dobashi Yoh, Hashimoto Ritsuo
Department of Neurology, International University of Health and Welfare Hospital, 537-3, Iguchi, Nasushiobara, Tochigi 329-2763, Japan.
Department of Pathology, International University of Health and Welfare Hospital, 537-3, Iguchi, Nasushiobara, Tochigi 329-2763, Japan.
J Clin Med Res. 2024 Sep;16(9):440-448. doi: 10.14740/jocmr5273. Epub 2024 Sep 4.
Granulomatosis with polyangiitis (GPA) has three clinicopathological features, namely, necrotizing granulomatosis of the upper respiratory tract and lungs, focal segmental necrotizing glomerulonephritis of the kidney, and necrotizing vasculitis of small vessels throughout the body. A 92-year-old man with clinically diagnosed probable Alzheimer's disease (AD) exhibited subacute deterioration in cognitive function. On admission, he was diagnosed with acute renal failure with an elevated creatinine level (5.48 mg/dL) as well as severe disturbance of consciousness. Antineutrophil cytoplasmic antibodies (ANCAs) directed against proteinase 3 (PR3-ANCA) were highly positive with ≥ 350 U/mL. The patient was diagnosed with GPA and was managed with steroid pulse therapy. However, he died without any improvement in renal function. As a result of the autopsy, the patient was diagnosed with definite AD, and his impaired consciousness was found not to be caused by central nervous system involvement due to GPA. As necrotizing crescentic glomerulonephritis was observed, the cause of the acute progressive renal failure was found to be PR3-ANCA-positive GPA. The autopsy revealed no GPA-related lesions in other parts of the body aside from the kidneys. It is rare to encounter cases of PR3-ANCA-positive GPA with renal-limited vasculitis and acute renal failure as the initial manifestation, as in the present case. Making an accurate clinical diagnosis of older patients suffering from various diseases in multiple organs is challenging. Although autopsy has the limitation of a terminal image, it is extremely useful in elucidating the pathophysiology of the older patient in this case.
肉芽肿性多血管炎(GPA)有三个临床病理特征,即上呼吸道和肺部的坏死性肉芽肿、肾脏的局灶节段性坏死性肾小球肾炎以及全身小血管的坏死性血管炎。一名临床诊断为可能患有阿尔茨海默病(AD)的92岁男性出现认知功能亚急性恶化。入院时,他被诊断为急性肾衰竭,肌酐水平升高(5.48mg/dL),还伴有严重意识障碍。抗蛋白酶3的抗中性粒细胞胞浆抗体(PR3-ANCA)≥350U/mL,呈高度阳性。该患者被诊断为GPA,并接受了类固醇脉冲治疗。然而,他的肾功能没有任何改善,最终死亡。尸检结果显示,该患者被确诊为明确的AD,其意识障碍并非由GPA累及中枢神经系统所致。由于观察到坏死性新月体性肾小球肾炎,发现急性进行性肾衰竭的病因是PR3-ANCA阳性的GPA。尸检显示,除肾脏外,身体其他部位未发现与GPA相关的病变。如本例所示,以肾脏局限性血管炎和急性肾衰竭为首发表现的PR3-ANCA阳性GPA病例较为罕见。对患有多种器官疾病的老年患者进行准确的临床诊断具有挑战性。尽管尸检有终末期图像的局限性,但在阐明本例老年患者的病理生理学方面非常有用。