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黏多糖贮积症 II 型的诊断与治疗。

The diagnosis and management of mucopolysaccharidosis type II.

机构信息

Department of Endocrinology, Children's Hospital of Zhejiang University School of Medicine, Hangzhou, China.

出版信息

Ital J Pediatr. 2024 Oct 8;50(1):207. doi: 10.1186/s13052-024-01769-9.

Abstract

Mucopolysaccharidosis type II (MPS II) is a rare X-linked recessive inherited lysosomal storage disease. With pathogenic variants of the IDS gene, the activity of iduronate-2-sulfatase (IDS) is reduced or lost, causing the inability to degrade glycosaminoglycans (GAGs) in cells and influencing cell function, eventually resulting in multisystemic manifestations, such as a coarse face, dysostosis multiplex, recurrent respiratory tract infections, and hernias. Diagnosing MPS II requires a combination of clinical manifestations, imaging examinations, urinary GAGs screening, enzyme activity, and genetic testing. Currently, symptomatic treatment is the main therapeutic approach. Owing to economic and drug availability issues, only a minority of patients opt for enzyme replacement therapy or hematopoietic stem cell transplantation. The limited awareness of the disease, the lack of widespread detection technology, and uneven economic development contribute to the high rates of misdiagnosis and missed diagnosis in China.

摘要

黏多糖贮积症 II 型(MPS II)是一种罕见的 X 连锁隐性遗传性溶酶体贮积病。由于 IDS 基因的致病变异,艾度糖-2-硫酸酯酶(IDS)的活性降低或丧失,导致细胞内糖胺聚糖(GAGs)无法降解,并影响细胞功能,最终导致多系统表现,如粗糙面容、多发性骨发育不良、反复呼吸道感染和疝气。MPS II 的诊断需要结合临床表现、影像学检查、尿 GAGs 筛查、酶活性和基因检测。目前,对症治疗是主要的治疗方法。由于经济和药物供应问题,只有少数患者选择酶替代疗法或造血干细胞移植。由于对该疾病的认识有限,广泛检测技术的缺乏以及经济发展的不平衡,导致中国误诊和漏诊率较高。

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