Hayashi Atsuko, Yamamoto Yasuji, Matsuda Minoru
Department of Rehabilitation Science, Kobe University Graduate School of Health Sciences, Kobe, JPN.
Department of Biosignal Pathophysiology, Kobe University Graduate School of Medicine, Kobe, JPN.
Cureus. 2024 Sep 23;16(9):e70045. doi: 10.7759/cureus.70045. eCollection 2024 Sep.
Primary progressive aphasia (PPA) is classified into several types. However, syndromes that do not belong to these typical types of PPA have been reported, such as cases where only progressive apraxia of speech (AOS) is present in the early stages of the disease. Moreover, there have been a few case reports of patients with progressive word deafness complicated with logoclonia as a speech disorder. Herein, we report a case of degenerative disease with phonological paraphasia, AOS, impaired speech sound cognition, and logoclonia with disease progression. The written language comprehension of the patient was superior to that of spoken language, and she could communicate in writing. She was neurologically normal; had no apraxia, agnosia, or memory impairment; and was independent in activities of daily living. Although she had moderate hearing loss, her speech-related hearing loss was disproportionately high. In analyses of brain imaging, dilation of the left Sylvian fissure, atrophy, and hypoperfusion of the superior temporal gyrus were prominent, and hypoperfusion of the left lateral frontal lobe was observed. Cerebrospinal fluid examination suggested that Alzheimer's disease (AD) pathology was unlikely, and decreased uptake was observed on a dopamine-active transporter scan. Word deafness was thought to be the most likely cause of the dissociation between spoken and written language in our patient. Our case and previous studies suggested that there is a syndrome presenting word deafness and speech movement disorders among patients with progressive communication disorders as a different entity from PPA. Although patients with this syndrome may experience agrammatism, inner language disorders are generally not as severe, and disorders in areas closer to the primary area, such as the motor and auditory areas, as well as cortical and subcortical disorders, are involved in this syndrome.
原发性进行性失语(PPA)可分为几种类型。然而,已有报道称存在不属于这些典型PPA类型的综合征,例如在疾病早期仅出现进行性言语失用(AOS)的病例。此外,也有少数关于进行性词聋合并言语重复症作为言语障碍的病例报告。在此,我们报告一例退行性疾病患者,其随着疾病进展出现音韵性错语、AOS、言语声音认知受损及言语重复症。患者的书面语言理解能力优于口语,她能够通过书写进行交流。她神经系统正常;无失用症、失认症或记忆障碍;日常生活活动能够自理。虽然她有中度听力损失,但与言语相关的听力损失比例过高。在脑成像分析中,左侧外侧裂增宽、颞上回萎缩和灌注不足较为明显,左侧额叶外侧也观察到灌注不足。脑脊液检查提示不太可能存在阿尔茨海默病(AD)病理改变,多巴胺活性转运体扫描显示摄取减少。词聋被认为是我们患者口语和书面语言分离的最可能原因。我们的病例及既往研究表明,在进行性交流障碍患者中存在一种以词聋和言语运动障碍为表现的综合征,它是一种与PPA不同的疾病实体。虽然患有这种综合征的患者可能会出现语法缺失,但内心语言障碍通常不那么严重,并且该综合征涉及更靠近初级区域的区域,如运动和听觉区域,以及皮质和皮质下的功能障碍。