Colloby Sean J, McAleese Kirsty E, Walker Lauren, Erskine Daniel, Toledo Jon B, Donaghy Paul C, McKeith Ian G, Thomas Alan J, Attems Johannes, Taylor John-Paul
Faculty of Medical Sciences, Translational and Clinical Research Institute, Newcastle University, Campus for Ageing and Vitality, Newcastle upon Tyne NE4 5PL, UK.
Stanley H. Appel Department of Neurology, Nantz National Alzheimer Center, Houston Methodist Hospital, Houston, TX 77030, USA.
Brain. 2025 May 13;148(5):1562-1576. doi: 10.1093/brain/awae372.
Alzheimer's disease (AD) is neuropathologically defined by deposits of misfolded hyperphosphorylated tau (HP-tau) and amyloid-β. Lewy body (LB) dementia, which includes dementia with Lewy bodies (DLB) and Parkinson's disease dementia (PDD), is characterized pathologically by α-synuclein aggregates. HP-tau and amyloid-β can also occur as co-pathologies in LB dementia, and a diagnosis of mixedAD/DLB can be made if present in sufficient quantities. We hypothesized that the spread of these abnormal proteins selectively affects vulnerable areas, resulting in pathologic regional covariance that differentially associates with pre-mortem clinical characteristics. Our aims were to map regional quantitative pathology (HP-tau, amyloid-β, α-synuclein) and investigate the spatial distributions from tissue microarray post-mortem samples across healthy aging, AD and LB dementia. The study involved 159 clinico-pathologically diagnosed human post-mortem brains (48 controls, 47 AD, 25 DLB, 20 mixedAD/DLB, 19 PDD). The burden of HP-tau, amyloid-β and α-synuclein was quantitatively assessed in cortical and subcortical areas. Principal components (PC) analysis was applied across all cases to determine the pattern nature of HP-tau, amyloid-β and α-synuclein. Further analyses explored the relationships of these pathological patterns with cognitive and symptom variables. Cortical (tauPC1) and temporo-limbic (tauPC2) patterns were observed for HP-tau. For amyloid-β, a cortical-subcortical pattern (amylPC1) was identified. For α-synuclein, four patterns emerged: 'posterior temporal-occipital' (synPC1), 'anterior temporal-frontal' (synPC2), 'parieto-cingulate-insula' (synPC3), and 'frontostriatal-amygdala' (synPC4). Distinct synPC scores were apparent among DLB, mixedAD/DLB and PDD, and may relate to different spreading patterns of α-synuclein pathology. In dementia, cognitive measures correlated with tauPC1,tauPC2 and amylPC1 pattern scores (P ≤ 0.02), whereas such variables did not relate to α-synuclein parameters in these or combined LB dementia cases. Mediation analysis then revealed that in the presence of amylPC1, tauPC1 had a direct effect on global cognition in dementia (n = 65, P = 0.04), while tauPC1 mediated the relationship between amylPC1 and cognition through the indirect pathway (amylPC1 → tauPC1 → global cognition) (P < 0.05). Last, in synucleinopathies, synPC1 and synPC4 pattern scores were associated with visual hallucinations and motor impairment, respectively (P = 0.02). In conclusion, distinct patterns of α-synuclein pathology were apparent in LB dementia, which could explain some of the disease heterogeneity and differing spreading patterns among these conditions. Visual hallucinations and motor severity were associated with specific α-synuclein topographies in LB dementia that may be important to the clinical phenotype and could, after necessary testing/validation, be integrated into semiquantitative routine pathological assessment.
阿尔茨海默病(AD)在神经病理学上的定义是由错误折叠的高磷酸化tau蛋白(HP-tau)和淀粉样β蛋白沉积所致。路易体(LB)痴呆,包括路易体痴呆(DLB)和帕金森病痴呆(PDD),在病理学上的特征是α-突触核蛋白聚集。HP-tau和淀粉样β蛋白也可作为LB痴呆的共同病理出现,如果数量足够,则可做出混合性AD/DLB的诊断。我们假设这些异常蛋白的扩散会选择性地影响易损区域,导致病理区域协方差,这与生前临床特征存在差异关联。我们的目的是绘制区域定量病理学图谱(HP-tau蛋白、淀粉样β蛋白、α-突触核蛋白),并研究来自健康衰老、AD和LB痴呆患者尸检组织微阵列样本的空间分布。该研究涉及159例经临床病理诊断的人类尸检大脑(48例对照、47例AD、25例DLB、20例混合性AD/DLB、19例PDD)。对皮质和皮质下区域的HP-tau蛋白、淀粉样β蛋白和α-突触核蛋白负担进行了定量评估。对所有病例进行主成分(PC)分析,以确定HP-tau蛋白、淀粉样β蛋白和α-突触核蛋白的模式性质。进一步的分析探讨了这些病理模式与认知和症状变量之间的关系。观察到HP-tau蛋白的皮质(tauPC1)和颞叶边缘(tauPC2)模式。对于淀粉样β蛋白,识别出一种皮质-皮质下模式(amylPC1)。对于α-突触核蛋白,出现了四种模式:“颞后枕叶”(synPC1)、“颞前额叶”(synPC2)、“顶叶扣带回岛叶”(synPC3)和“额纹状体杏仁核”(synPC4)。在DLB、混合性AD/DLB和PDD中,不同的synPC评分很明显,可能与α-突触核蛋白病理的不同扩散模式有关。在痴呆症中,认知测量与tauPC1、tauPC2和amylPC1模式评分相关(P≤0.02),而在这些病例或合并的LB痴呆病例中,这些变量与α-突触核蛋白参数无关。中介分析随后显示,在存在amylPC1的情况下,tauPC1对痴呆症的整体认知有直接影响(n = 65,P = 0.04),而tauPC1通过间接途径介导amylPC1与认知之间的关系(amylPC1→tauPC1→整体认知)(P < 0.05)。最后,在突触核蛋白病中,synPC1和synPC4模式评分分别与视幻觉和运动障碍相关(P = 0.02)。总之,在LB痴呆中,α-突触核蛋白病理的不同模式很明显,这可以解释这些疾病的一些异质性以及这些情况下不同的扩散模式。视幻觉和运动严重程度与LB痴呆中特定的α-突触核蛋白拓扑结构相关,这可能对临床表型很重要,并且在经过必要的测试/验证后,可以纳入半定量常规病理评估中。