Saburi Masuho, Nishikawa Takumi, Maehara Kuniaki, Uraisami Keiichi, Takata Hiroyuki, Miyazaki Yasuhiko, Narahara Kumiko, Sasaki Hitohiro, Abe Miyuki, Kohno Kazuhiro, Nakayama Toshiyuki, Ohtsuka Eiichi
Department of Hematology, Oita Prefectural Hospital, Oita, JPN.
Department of Hematology, Oita Kouseiren Tsurumi Hospital, Oita, JPN.
Cureus. 2024 Nov 19;16(11):e73988. doi: 10.7759/cureus.73988. eCollection 2024 Nov.
Background and objective There is scarce data on the treatment outcomes of B-cell acute lymphoblastic leukemia/lymphoblastic lymphoma (B-ALL/LBL) in elderly patients in the era of tyrosine kinase inhibitors (TKIs), blinatumomab, and inotuzumab ozogamicin. In light of this, we aimed to address this gap in data by conducting this retrospective study. Methods Treatment outcomes were retrospectively evaluated by using data from transplant-ineligible patients aged 65 years or older with newly diagnosed B-ALL/LBL (n=29) at two hospitals in Oita, Japan between 2013 and 2023. Results The median age of the cohort was 72 (65-88) years, and 10 patients were male; 17 patients had Philadelphia chromosome (Ph)-positive ALL, and the others had Ph-negative ALL. Dasatinib combined with prednisolone was the most common induction therapy for Ph-positive ALL (88.2%). Complete response (CR) was achieved in 93.1%, and the CR rate did not differ significantly between Ph-positive ALL (100%) and Ph-negative ALL (83.3%) (p=0.16). The median observation period was 1.52 (range: 0.03-8.98) years. Overall survival (OS) and event-free survival (EFS) were significantly longer in Ph-positive ALL patients than in Ph-negative ALL patients on univariate analysis (OS: p=0.011, EFS: p=0.041). Multivariate analyses showed that the presence of Ph was significantly and independently associated with longer OS [hazard ratio (HR): 0.29, 95% confidence interval (CI): 0.10-0.87, p=0.027] and EFS (HR: 0.34, 95% CI: 0.12-0.91, p=0.03). There was no difference in relapse-free survival (RFS); 13 patients (76.5%) with Ph-positive ALL were treated with ponatinib (salvage therapy, n=7; consolidation or maintenance therapy in CR, n=6). Six of seven patients (85.7%) with ponatinib salvage therapy achieved CR, and all six patients treated with ponatinib consolidation or maintenance therapy retained CR at the last follow-up. Six patients (Ph-positive ALL: n=4; Ph-negative ALL: n=2) were treated with blinatumomab, including salvage therapy for primary refractory or relapse (n=3), and consolidation therapy due to intolerance to conventional chemotherapies (n=3). Two of three patients with blinatumomab salvage therapy achieved CR, and all three patients with blinatumomab consolidation therapy maintained CR in follow-up. Two patients (Ph-positive ALL: n=1; Ph-negative ALL: n=1) were treated with inotuzumab ozogamicin for relapsed or refractory ALL. A patient with Ph-positive ALL for the third relapse achieved CR, which was sustained for three years. The other patient with Ph-negative ALL for primary refractory achieved CR but relapsed after the fourth course of inotuzumab ozogamicin. Conclusions Elderly patients with Ph-positive ALL showed significantly longer OS and EFS than those with Ph-negative ALL in the era of molecular-targeted therapy.
背景与目的 在酪氨酸激酶抑制剂(TKIs)、博纳吐单抗和伊奈妥单抗时代,老年B细胞急性淋巴细胞白血病/淋巴细胞淋巴瘤(B-ALL/LBL)患者的治疗结局数据稀缺。鉴于此,我们旨在通过开展这项回顾性研究来填补这一数据空白。方法 利用2013年至2023年期间日本大分县两家医院新诊断为B-ALL/LBL的65岁及以上不适合移植患者(n = 29)的数据,对治疗结局进行回顾性评估。结果 该队列的中位年龄为72(65 - 88)岁,男性10例;17例患者为费城染色体(Ph)阳性ALL,其余为Ph阴性ALL。达沙替尼联合泼尼松龙是Ph阳性ALL最常见的诱导治疗方案(88.2%)。完全缓解(CR)率为93.1%,Ph阳性ALL(100%)和Ph阴性ALL(83.3%)之间的CR率无显著差异(p = 0.16)。中位观察期为1.52(范围:0.03 - 8.98)年。单因素分析显示,Ph阳性ALL患者的总生存期(OS)和无事件生存期(EFS)显著长于Ph阴性ALL患者(OS:p = 0.011,EFS:p = 0.041)。多因素分析表明,Ph的存在与更长的OS [风险比(HR):0.29,95%置信区间(CI):0.10 - 0.87,p = 0.027]和EFS(HR:0.34,95% CI:0.12 - 0.91,p = 0.03)显著且独立相关。无复发生存期(RFS)无差异;13例(76.5%)Ph阳性ALL患者接受了波纳替尼治疗(挽救治疗,n = 7;CR期巩固或维持治疗,n = 6)。7例接受波纳替尼挽救治疗的患者中有6例(85.7%)达到CR,所有6例接受波纳替尼巩固或维持治疗的患者在最后一次随访时仍保持CR。6例患者(Ph阳性ALL:n = 4;Ph阴性ALL:n = 2)接受了博纳吐单抗治疗,包括原发性难治或复发的挽救治疗(n = 3)以及因不耐受传统化疗而进行的巩固治疗(n = 3)。3例接受博纳吐单抗挽救治疗的患者中有2例达到CR,所有3例接受博纳吐单抗巩固治疗的患者在随访中均维持CR。2例患者(Ph阳性ALL:n = 1;Ph阴性ALL:n = 1)因复发或难治性ALL接受了伊奈妥单抗治疗。1例Ph阳性ALL第三次复发患者达到CR,并持续了三年。另1例Ph阴性ALL原发性难治患者达到CR,但在伊奈妥单抗治疗的第四个疗程后复发。结论 在分子靶向治疗时代,Ph阳性ALL老年患者的OS和EFS显著长于Ph阴性ALL老年患者。