Kawamura Junpei, Yamakuchi Munekazu, Ueno Kentaro, Hashiguchi Teruto, Okamoto Yasuhiro
Department of Pediatrics, Graduate School of Medical and Dental Sciences, Kagoshima University, Kagoshima, Japan.
Department of Laboratory and Vascular Medicine, Graduate School of Medical and Dental Sciences, Kagoshima University, Kagoshima, 890-8544, Japan.
Sci Rep. 2025 Feb 3;15(1):4138. doi: 10.1038/s41598-025-88840-5.
The detailed mechanism of pulmonary arteriovenous malformations after Glenn surgery (G-PAVMs) in cyanotic congenital heart disease (CHD) remains unclear. Microarray in situ hybridization was performed to assess the miRNA (miRNA) profiles of serum from pediatric patients (0-6 years of age) with G-PAVMs and after the Fontan procedure without G-PAVMs. In addition, we investigated the tube formation, migration, and proliferation of human lung microvascular endothelial cells (HMVEC-L) transfected with miR-25-3p mimic, miR-25-3p inhibitor, or PHLPP2 small interfering RNA, and examined HIF-1α/VEGF-A signaling after hypoxic stimulation. Serum miRNAs that showed ≥ 2-fold higher levels in patients with G-PAVMs than in other patients were selected. MiR-25-3p was significantly upregulated in the pulmonary artery sera of the post-Glenn group than in the post-Fontan group. We identified PHLPP2 as a direct target of miR-25-3p. PHLPP2 expression was significantly decreased in HMVEC-L transfected with miR-25-3p mimic compared to the control cells. HIF-1α and VEGF-A expression levels were increased in HMVEC-L transfected with miR-25-3p mimic compared to the control cells in a PHLPP2/Akt/mTOR signaling-dependent manner after hypoxic stimulation. MiR-25-3p promoted HMVEC-L angiogenesis, proliferation, and migration under hypoxic conditions. MiR-25-3p in the pulmonary arteries may contribute to G-PAVM development.
紫绀型先天性心脏病(CHD)患者在格林手术(G-PAVM)后发生肺动静脉畸形的详细机制仍不清楚。进行了微阵列原位杂交,以评估患有G-PAVM的小儿患者(0至6岁)以及在进行Fontan手术但无G-PAVM的小儿患者血清中的微小RNA(miRNA)谱。此外,我们研究了用miR-25-3p模拟物、miR-25-3p抑制剂或PHLPP2小干扰RNA转染的人肺微血管内皮细胞(HMVEC-L)的管形成、迁移和增殖,并在缺氧刺激后检测了HIF-1α/VEGF-A信号传导。选择了在患有G-PAVM的患者中血清miRNA水平比其他患者高至少2倍的miRNA。与Fontan术后组相比,miR-25-3p在格林术后组的肺动脉血清中显著上调。我们确定PHLPP2是miR-25-3p的直接靶点。与对照细胞相比,用miR-25-3p模拟物转染的HMVEC-L中PHLPP2表达显著降低。在缺氧刺激后,与对照细胞相比,用miR-25-3p模拟物转染的HMVEC-L中HIF-1α和VEGF-A表达水平以PHLPP2/Akt/mTOR信号传导依赖性方式增加。在缺氧条件下,miR-25-3p促进HMVEC-L血管生成、增殖和迁移。肺动脉中的miR-25-3p可能促成G-PAVM的发展。