Nevarez Gilbert Ana, Rahde Bischoff Adrianne, Merrill Kyle
Division of Neonatology, University of Iowa Stead Family Children's Hospital, Iowa City, Iowa, USA.
Division of Nephrology, Dialysis and Transplantation, University of Iowa Stead Family Children's Hospital, Iowa City, Iowa, USA.
Case Rep Nephrol. 2025 Mar 24;2025:1431773. doi: 10.1155/crin/1431773. eCollection 2025.
Autosomal recessive polycystic kidney disease (ARPKD) is a form of hereditary cystic disease with a highly variable phenotypic expression that ultimately leads to chronic kidney disease. Severe cases may warrant surgical intervention with unilateral or bilateral nephrectomy to alleviate thoracic and abdominal compression from massive nephromegaly. Hypotension has been identified as a potential complication following nephrectomy in pediatric patients. We present the case of an infant with end-stage kidney disease secondary to ARPKD who developed refractory hypotension following elective bilateral nephrectomies. We describe the use of angiotensin-II infusion with a significant increase in mean arterial blood pressure and successful reduction in other inotropic and vasopressor support. This case suggests that angiotensin-II may represent another valuable therapeutic agent in the treatment of refractory hypotension in anephric infants.
常染色体隐性多囊肾病(ARPKD)是一种遗传性囊性疾病,其表型表达高度可变,最终会导致慢性肾病。严重病例可能需要进行单侧或双侧肾切除术的手术干预,以缓解巨大肾肿大引起的胸腹部压迫。低血压已被确认为儿科患者肾切除术后的一种潜在并发症。我们报告了一例因ARPKD继发终末期肾病的婴儿,在择期双侧肾切除术后出现难治性低血压的病例。我们描述了使用血管紧张素II输注后平均动脉血压显著升高,以及其他正性肌力药和血管升压药支持成功减少的情况。该病例表明,血管紧张素II可能是治疗无肾婴儿难治性低血压的另一种有价值的治疗药物。