Vahedi Matin, Rad Ali Motamedi, Nazar Elham, Samimiat Alireza
Department of General Surgery, Sina Hospital, Tehran University of Medical Sciences, Tehran, Iran.
School of Medicine, Tehran University of Medical Sciences, Tehran, Iran.
Int J Surg Case Rep. 2025 May;130:111235. doi: 10.1016/j.ijscr.2025.111235. Epub 2025 Mar 29.
Bronchogenic cysts are rare congenital malformations of the respiratory tract, arising from abnormal budding of the foregut during embryogenesis. Clinical manifestations vary by location and complications, ranging from asymptomatic to causing respiratory distress in newborns or recurrent respiratory issues in adults. Subdiaphragmatic bronchogenic cysts are extremely rare, with only a limited number of case reports published. They often present without symptoms or with nonspecific symptoms such as abdominal pain. Diagnosis typically relies on histopathologic analysis of excised biopsies performed during surgery. Due to their rarity and lack of distinctive clinical features, these cysts pose significant diagnostic challenges.
A 36-year-old Iranian man, presented with a 5-month history of abdominal pain. Abdominal sonography revealed a cystic lesion posterior to the liver. An aspiration biopsy indicated an inflammatory process. An abdominal CT scan without contrast reported a right subdiaphragmatic cyst measuring 68 × 52 × 48 mm with a pressure effect on the liver. The diagnosis was uncertain. The cyst was surgically removed, and histopathologic studies confirmed it to be a bronchogenic cyst. The patient had an uneventful recovery with no recurrence after six months.
In addition to presenting our case report, we reviewed recent literature and added 24 new cases to the previously identified 100 cases of subdiaphragmatic bronchogenic cysts. Subdiaphragmatic bronchogenic cysts are rare lesions with no specific presentation, making diagnosis extremely challenging.
SBC is a benign lesion. Most patients are asymptomatic; however, due to the favorable prognosis following resection surgery, it remains the optimal management strategy.
支气管源性囊肿是呼吸道罕见的先天性畸形,由胚胎发育过程中前肠的异常芽生引起。临床表现因位置和并发症而异,从无症状到导致新生儿呼吸窘迫或成人反复出现呼吸道问题。膈下支气管源性囊肿极为罕见,仅有有限数量的病例报告发表。它们通常无症状或表现为腹痛等非特异性症状。诊断通常依赖于手术期间切除活检的组织病理学分析。由于其罕见性和缺乏独特的临床特征,这些囊肿带来了重大的诊断挑战。
一名36岁的伊朗男性,有5个月的腹痛病史。腹部超声检查发现肝脏后方有一个囊性病变。穿刺活检显示为炎症过程。未增强的腹部CT扫描报告右膈下有一个68×52×48mm的囊肿,对肝脏有压迫效应。诊断不确定。该囊肿经手术切除,组织病理学研究证实为支气管源性囊肿。患者恢复顺利,六个月后无复发。
除了展示我们的病例报告外,我们还回顾了近期文献,并在先前确定的100例膈下支气管源性囊肿病例基础上增加了24例新病例。膈下支气管源性囊肿是罕见病变,无特异性表现,诊断极具挑战性。
膈下支气管源性囊肿是一种良性病变。大多数患者无症状;然而,由于切除手术后预后良好,手术仍是最佳治疗策略。